Kasamatsu Daigo, Tsunemitsu Takefumi, Matsumoto Masaru, Suzuki Takao
Department of Emergency and Critical Care Medicine, Hyogo Prefectural Amagasaki General Medical Center, Amagasaki, JPN.
Department of Preventive Services, School of Public Health, Kyoto University Graduate School of Medicine, Kyoto, JPN.
Cureus. 2025 Jul 24;17(7):e88700. doi: 10.7759/cureus.88700. eCollection 2025 Jul.
Osmotic demyelination syndrome (ODS) is typically associated with rapid correction of severe hyponatremia but is a rare complication of hyperosmolar hyperglycemic state (HHS). We describe two cases of ODS developing in HHS with contrasting initial sodium levels: one with profound hyponatremia (Na 112 mmol/L, corrected 167 mmol/L) and the other with hypernatremia (Na 149 mmol/L, corrected 177 mmol/L). Both patients exhibited severe hyperglycemia (2,398 and 1,277 mg/dL, respectively) and marked hyperosmolality (387 and 421 mOsm/kg) and were managed with cautious correction rates (1.2 and 1.0 mOsm/kg/hour). Despite this, each patient developed ODS diagnosed by MRI on days three and seven, respectively. Neurological function gradually improved in both, with final modified Rankin Scale scores of 2 and 1, respectively. To our knowledge, this is the first case report to directly compare hyponatremic and hypernatremic ODS in the context of HHS. Severe hyperosmolality can itself trigger ODS, regardless of measured and corrected sodium levels or the rate of correction. Clinicians should maintain a low threshold for timely MRI in HHS patients with persistent or unexplained neurological deficits.
渗透性脱髓鞘综合征(ODS)通常与严重低钠血症的快速纠正相关,但却是高渗高血糖状态(HHS)的一种罕见并发症。我们描述了两例在HHS中发生的ODS病例,其初始钠水平形成对比:一例为严重低钠血症(血钠112 mmol/L,纠正后167 mmol/L),另一例为高钠血症(血钠149 mmol/L,纠正后177 mmol/L)。两名患者均表现出严重高血糖(分别为2398和1277 mg/dL)和显著高渗状态(分别为387和421 mOsm/kg),并以谨慎的纠正速率(分别为1.2和1.0 mOsm/kg/小时)进行处理。尽管如此,两名患者分别在第3天和第7天经MRI诊断为ODS。两人的神经功能均逐渐改善,最终改良Rankin量表评分分别为2分和1分。据我们所知,这是第一例在HHS背景下直接比较低钠血症性和高钠血症性ODS的病例报告。严重高渗状态本身可引发ODS,无论测得的和纠正后的钠水平或纠正速率如何。对于有持续或不明原因神经功能缺损的HHS患者,临床医生应保持较低的阈值以便及时进行MRI检查。