Wolfson David W, Hull Joshua A, Li Yongwu, Gonzalez Trevor J, Jayaram Mourya D, Devlin Garth W, Cigliola Valentina, Oonk Kelsey A, Rosales Alan, Bursac Nenad, Asokan Aravind, Poss Kenneth D
Department of Cell Biology, Duke Regeneration Center, Duke University School of Medicine, Durham, United States.
Department of Surgery, Duke University School of Medicine, Durham, United States.
Elife. 2025 Sep 12;14:RP107148. doi: 10.7554/eLife.107148.
Tissue regeneration enhancer elements (TREEs) direct expression of target genes in injured and regenerating tissues. Additionally, TREEs of zebrafish origin were shown to direct expression of transgenes in border zone regions after cardiac injury when packaged into recombinant adeno-associated viral (AAV) vectors and introduced into mice. Future implementation of TREEs into AAV-based vectors as research tools and potential gene therapy modalities requires a deeper understanding of expression dynamics and potential off-target effects. Here, we applied in vivo bioluminescent imaging to mice systemically injected with AAV vectors containing different combinations of capsids, enhancers, and timing of delivery. Longitudinal tracking of expression directed by different TREEs revealed distinct amplitudes and durations of reporter gene expression in the injured heart. The liver-de-targeted AAV capsid, AAV.cc84, could deliver TREEs either pre- or post-cardiac injury to negate off-target expression in the liver while maintaining transduction in the heart. By screening AAV9-based capsid libraries dosed systemically in mice post-cardiac injury, we discovered a new capsid variant, AAV.IR41, with enhanced transduction in cardiac injuries and with elevated transduction of TREE-driven transgenes versus conventional AAV9 vectors. In vivo bioluminescence imaging offers insights into how enhancers and engineered capsids can be implemented to modulate spatiotemporal transgene expression for targeted therapies.
组织再生增强元件(TREEs)可指导靶基因在损伤和再生组织中的表达。此外,当包装到重组腺相关病毒(AAV)载体中并引入小鼠体内时,源自斑马鱼的TREEs可指导转基因在心脏损伤后的边界区域表达。将TREEs应用于基于AAV的载体作为研究工具和潜在的基因治疗方式,需要更深入地了解表达动态和潜在的脱靶效应。在此,我们对全身注射含有不同衣壳、增强子和递送时间组合的AAV载体的小鼠应用了体内生物发光成像技术。对不同TREEs指导的表达进行纵向跟踪,揭示了损伤心脏中报告基因表达的不同幅度和持续时间。肝脏脱靶的AAV衣壳AAV.cc84可在心脏损伤前或损伤后递送TREEs,以消除肝脏中的脱靶表达,同时维持心脏中的转导。通过筛选心脏损伤后全身给药的基于AAV9的衣壳文库,我们发现了一种新的衣壳变体AAV.IR41,与传统的AAV9载体相比,它在心脏损伤中的转导增强,并且TREE驱动的转基因的转导也有所提高。体内生物发光成像为如何利用增强子和工程化衣壳来调节时空转基因表达以实现靶向治疗提供了见解。