Delâge J M, Bergeron P, Simard J, Lehner-Netsch G, Prochazka E
J Clin Invest. 1977 Nov;60(5):1061-9. doi: 10.1172/JCI108857.
The serum of a 44-yr-old woman of French-Canadian descent having a B-27 positive ankylosing spondylitis was deficient in the seventh component of complement (C7) as determined by hemolytic and immunochemical methods. No inhibitor against C7 was detected, and the levels of all other complement components were normal. No deficiency in the opsonic activity of the serum was found, and the results of basic coagulation studies of the plasma were normal. On investigation of the patient's family, two sisters were found to have the same deficiency but were otherwise in good health. The seven other siblings were heterozygous for C7 deficiency, while the paternal aunt had a normal C7 level. In the third generation, six children of the three homozygous sisters and five children of heterozygotes were available for testing. Studies of the HLA antigens in all the 22 subjects and in three spouses indicated no close linkage between the CM deficienty and the HLA system. In addition, the simultaneous occurrence of two hereditary complement deficiencies (C2 and C7) was discovered in one family of this remarkable kindred.
一名44岁法裔加拿大血统女性,患B-27阳性强直性脊柱炎,其血清经溶血和免疫化学方法测定,补体第七成分(C7)缺乏。未检测到针对C7的抑制剂,所有其他补体成分水平正常。未发现血清调理活性缺乏,血浆基础凝血研究结果正常。对患者家族进行调查时发现,两名姐妹有相同的缺乏情况,但其他方面健康状况良好。其他七个兄弟姐妹为C7缺乏杂合子,而其姑姑C7水平正常。在第三代中,三名纯合子姐妹的六个孩子和杂合子的五个孩子可供检测。对所有22名受试者及三名配偶的HLA抗原研究表明,C7缺乏与HLA系统之间无紧密连锁关系。此外,在这个非凡的家族的一个家庭中发现了两种遗传性补体缺乏(C2和C7)同时出现的情况。