Elias Nardin, Armon Noam, Rittblat Mor
From the Department of Plastic and Reconstructive Surgery, Hadassah Hebrew University Medical Centre, Jerusalem, Israel.
Department of Military Medicine and "Tzameret," Faculty of Medicine, The Hebrew University of Jerusalem, Jerusalem, Israel.
Plast Reconstr Surg Glob Open. 2025 Sep 24;13(9):e7108. doi: 10.1097/GOX.0000000000007108. eCollection 2025 Sep.
Congenital lateral upper lip sinus is an exceptionally rare developmental anomaly, with few cases reported in the literature. It is characterized by the presence of a sinus tract located on the lateral aspect of the upper lip, which may lead to intermittent discharge and cosmetic concerns. Surgical excision is the standard treatment to prevent recurrence and restore lip contour.
We report a case of a 1-year-old male infant with a congenital lateral upper lip sinus, present since birth and associated with intermittent clear discharge. Clinical evaluation and ultrasonography were performed to assess the extent of the sinus tract. Surgical excision was undertaken under general anesthesia using a fine metal probe to delineate the tract and aid in dissection. The sinus tract was removed completely, and layered closure of the wound was performed.
The sinus tract measured approximately 2 cm in length and extended through the orbicularis oris muscle without involving deeper structures. Histopathologic analysis confirmed a tract lined by a stratified squamous epithelium. Postoperative recovery was uneventful, with no evidence of infection or recurrence at the 1-year follow-up. The aesthetic outcome was satisfactory with minimal scarring.
Although rare, congenital lateral upper lip sinus should be considered in the differential diagnosis of lip anomalies in infants. Early surgical intervention allows for definitive treatment with excellent cosmetic and functional outcomes. This case added to the limited literature and reinforced the importance of complete excision to prevent recurrence.
先天性外侧上唇窦是一种极为罕见的发育异常,文献报道的病例较少。其特征是上唇外侧存在一个窦道,可能导致间歇性分泌物排出及美观问题。手术切除是预防复发和恢复唇部外形的标准治疗方法。
我们报告一例1岁男性婴儿先天性外侧上唇窦病例,自出生即存在,伴有间歇性清亮分泌物排出。进行了临床评估和超声检查以评估窦道范围。在全身麻醉下使用细金属探针描绘窦道并辅助解剖,进行手术切除。完全切除窦道后,分层缝合伤口。
窦道长度约2厘米,穿过口轮匝肌,未累及更深层结构。组织病理学分析证实窦道内衬复层鳞状上皮。术后恢复顺利,1年随访时无感染或复发迹象。美学效果满意,瘢痕极小。
尽管罕见,但先天性外侧上唇窦应纳入婴儿唇部异常的鉴别诊断中。早期手术干预可实现确定性治疗,获得良好的美容和功能效果。该病例丰富了有限的文献资料,强化了完整切除以预防复发的重要性。