Smith I, Wolff O H
Lancet. 1974 Sep 7;2(7880):540-4. doi: 10.1016/s0140-6736(74)91873-x.
This study describes the intellectual development of twenty-eight sibling pairs with phenylketonuria in which the index case presented because of retarded development. In twelve pairs (group I) the "second" sibling was born subsequently, and in sixteen (group II) there was a second sibling already in the family at the time of diagnosis of the index case. The intellectual outcome of the second siblings of group II suggests that approximately 1 in 6 or 7 patients with untreated classical phenylketonuria achieves an I.Q. above 70, although with evidence of intellectual impairment. The highly significant difference in intellectual outcome between the early treated second siblings of group I and the late or untreated second siblings of group II demonstrates the beneficial effect of early treatment on the intelligence of affected children.
本研究描述了28对患苯丙酮尿症的同胞兄弟姐妹的智力发育情况,其中索引病例因发育迟缓就诊。在12对(第一组)中,“第二个”兄弟姐妹是随后出生的,在16对(第二组)中,在索引病例诊断时家中已有第二个兄弟姐妹。第二组中第二个兄弟姐妹的智力结果表明,未经治疗的典型苯丙酮尿症患者中,约每6或7人中有1人智商高于70,尽管有智力损害的证据。第一组早期接受治疗的第二个兄弟姐妹与第二组晚期或未接受治疗的第二个兄弟姐妹在智力结果上的高度显著差异,证明了早期治疗对患病儿童智力的有益影响。