Del Valle J A, Garcia M J, Merinero B, Pérez-Cerdá C, Roman F, Jimenez A, Ugarte M, Martínez-Pardo M, Ludeña C, Camarero C
J Inherit Metab Dis. 1984;7(2):62-4. doi: 10.1007/BF01805804.
A new patient with medium-chain dicarboxylic aciduria and suberyl glycinuria during an attack of acute illness is reported. When, inadvertently he was given medium-chain triglycerides for 2 days, the excretion of abnormal metabolites of medium-chain fatty acids increased and hepatomegaly became more pronounced. During remission a low excretion of the metabolites were observed. After 16 h of fasting hypoglycaemia was accompanied by an increase of urinary dicarboxylic acids and psi-hydroxyacids similar to that found on admission. Interestingly this urinary organic acid pattern persisted 8 h after intravenous administration of glucose. In a blood sample obtained after 16 h of fasting there was hypoketonaemia and increased levels of total free fatty acids, octanoic, decanoic and cis-4-decenoic acids. These biochemical data suggest the existence of a deficiency at the level of medium-chain acyl-CoA dehydrogenase.
报告了一名患有中链二羧酸尿症和辛二酰甘氨酸尿症的新患者在急性疾病发作期间的情况。在无意中给予他中链甘油三酯2天后,中链脂肪酸异常代谢产物的排泄增加,肝肿大变得更加明显。在缓解期观察到代谢产物排泄量较低。禁食16小时后出现低血糖,同时尿中二羧酸和ψ-羟基酸增加,与入院时情况相似。有趣的是,静脉注射葡萄糖8小时后,这种尿有机酸模式仍然存在。在禁食16小时后采集的血样中,出现了低酮血症,总游离脂肪酸、辛酸、癸酸和顺-4-癸烯酸水平升高。这些生化数据表明在中链酰基辅酶A脱氢酶水平存在缺陷。