Ricoy J R, Cabello A, Goizueta G
J Neurol Sci. 1980 Oct;48(1):81-92. doi: 10.1016/0022-510x(80)90152-5.
Two cases of non-progressive congenital hypotonia are described in siblings, male and female, aged 5 and 9 years, respectively, which morphologically correspond to myopathy with multicore or minicore. The study of these 2 cases is compared with those described in the literature, with special emphasis on the analysis of the histochemical picture. The disease in all the cases is defined by the presence of multiple small foci of loss of cross striation with loss of activity of myofibrillar ATPase and oxidative enzymes. Furthermore, a predominance and hypotrophy of type I fibers and in some cases hypertrophy of type II is constantly recorded, which is interpreted as an alteration in muscle maturation. We review other myopathies described with focal loss of cross-striation which associate central nuclei with the myofibrillar lesion, considering them to be myopathy with multicore or minicore.
本文描述了两例非进行性先天性肌张力减退病例,患者为兄妹,分别为5岁男性和9岁女性,形态学上与多核或小核肌病相符。将这2例病例的研究与文献中描述的病例进行了比较,特别强调了组织化学图像分析。所有病例的疾病特征均为存在多个横纹消失的小病灶,同时肌原纤维ATP酶和氧化酶活性丧失。此外,持续观察到I型纤维占优势且肥大,在某些情况下II型纤维也肥大,这被解释为肌肉成熟过程中的一种改变。我们回顾了其他伴有横纹局部消失的肌病,这些肌病将中央核与肌原纤维病变联系起来,认为它们是多核或小核肌病。