Wilson W G, Wyandt H E, Shah H
Am J Dis Child. 1983 May;137(5):444-8.
A patient with multiple exostoses, mental retardation, and unusual facies has an interstitial deletion of the long arm of chromosome 8, or 46,XX, del (8) (pter leads to q22::q24.1 leads to qter). She has some features of the Langer-Giedion syndrome, but her facies are not characteristic and she does not have cone-shaped phalangeal epiphyses. Of the eight previous reports of partial deletion of the long arm of chromosome 8, four patients had exostoses and unusual facies, three of whom had characteristics of the Langer-Gieldion syndrome. The deleted segments in the patients with exostoses are not identical, although there are areas of deletion that are seen in more than one patient. Among the explanations of the relationship of the 8q deletions to exostoses is the presence of several loci on 8q that are involved in bone formation, the deletion of any of which may give rise to a similar skeletal defect.
一名患有多发性外生骨疣、智力发育迟缓及特殊面容的患者存在8号染色体长臂的间质性缺失,核型为46,XX,del(8)(pter→q22::q24.1→qter)。她具有一些朗格-吉迪恩综合征的特征,但面容不典型,且没有锥形指骨骨骺。在之前八篇关于8号染色体长臂部分缺失的报告中,四名患者有外生骨疣和特殊面容,其中三名具有朗格-吉迪恩综合征的特征。有外生骨疣的患者中缺失片段并不相同,尽管有一些缺失区域在不止一名患者中出现。关于8q缺失与外生骨疣之间关系的解释包括8q上存在几个参与骨形成的基因座,其中任何一个基因座的缺失都可能导致类似的骨骼缺陷。