Schutgens R B, Beemer F A, Tegelaers W H, de Groot W P
J Inherit Metab Dis. 1980;2(1):13-4. doi: 10.1007/BF01805556.
A 7 and one half-year-old boy with a massive excretion of argininosuccinic acid is described. He exhibited only moderate mental retardation, cerebellar ataxia and both abnormal hair and skin. Argininosuccinate lyase activity in the erythrocytes of his parents and his sister was in the range expected for heterozygotes. The patient was put on a low protein diet with arginine supplementation and improved clinically and biochemically on this regime. The variability of the phenotypic expression of argininosuccinate lyase deficiency is stressed.
本文描述了一名7岁半的男孩,其精氨琥珀酸排泄量巨大。他仅表现出中度智力发育迟缓、小脑共济失调以及毛发和皮肤异常。其父母和姐姐红细胞中的精氨琥珀酸裂解酶活性处于杂合子预期范围内。该患者接受了低蛋白饮食并补充精氨酸,在此治疗方案下临床和生化指标均有所改善。强调了精氨琥珀酸裂解酶缺乏症表型表达的变异性。