Happle R
Hautarzt. 1982 Feb;33(2):73-81.
In X-linked inheritance, the difference between the terms dominant and recessive is blurred by the Lyon effect. In some X-linked recessive genodermatoses, the Lyon effect makes the detection of heterozygote females possible, either by clinical cromanifestations or by enzymatic demonstration of two functionally different populations of cells. The gene locus of X-linked recessive ichthyosis, however, escapes X-inactivation, but heterozygotes can be detected by enzyme analysis in this condition, too. X-linked dominant gene defects with manifestation in both sexes include keratosis follicularis spinulosa decalvans, and probably also the Bazex syndrome. The group of X-linked dominant gene defects with lethality in the male comprises incontinentia pigmenti, focal dermal hypoplasia, the oral-facial-digital syndrome and the CHILD syndrome. Prenatal diagnosis of severe X-linked conditions can be performed when the underlying defect of cell function is known (Fabry disease, Menkes syndrome). In other severe X-linked disorders, the possibility of prenatal determination of the sex may be considered (Wiskott-Aldrich syndrome, X-linked dominant chondrodysplasia punctata, oral-facial-digital syndrome).
在X连锁遗传中,莱昂效应模糊了显性和隐性这两个术语之间的区别。在一些X连锁隐性遗传性皮肤病中,莱昂效应使得通过临床表型或通过对两种功能不同的细胞群体进行酶学检测来检测杂合子女性成为可能。然而,X连锁隐性鱼鳞病的基因座逃避X染色体失活,但在这种情况下杂合子也可通过酶分析检测到。在两性中均有表现的X连锁显性基因缺陷包括毛囊角化病,可能还有巴泽克斯综合征。男性致死性的X连锁显性基因缺陷包括色素失禁症、局灶性真皮发育不全、口面指综合征和CHILD综合征。当细胞功能的潜在缺陷已知时(法布里病、门克斯综合征),可对严重的X连锁疾病进行产前诊断。在其他严重的X连锁疾病中,可考虑进行产前性别鉴定(威斯科特-奥尔德里奇综合征、X连锁显性点状软骨发育不良、口面指综合征)。