Kodet R, Smelhaus V, Newton W A, Hamoudi A B, Qualman S J, Singley C, Jacobs D L
Department of Pathology, 2nd Faculty of Medicine, Charles' University, Prague, Czech Republic.
Pediatr Pathol. 1994 May-Jun;14(3):433-51. doi: 10.3109/15513819409024274.
Epithelioid sarcoma in a rare tumor and most of the cases occur in young adults. It is rare in childhood. We have been able to obtain data and histologic material for 11 patients with this disease. The primary sites were head and neck in three patients, inguinal region in one, and extremities in seven. The age range of the patients was 12 weeks to 13 years. There was a preponderance of males over females with a ratio of 1.75. The tumors presented with a typical nodular necrotizing pattern. In three cases giant osteoclast-like cells were present. The immunohistochemistry and electron microscopy showed features consistent with previous observations on epithelioid sarcomas. In one case islands of small dark cells noted on light microscopy were surrounded by basal lamina on electron microscopy. The cells inside the nests were undifferentiated. Six tumors studied by flow cytometry were in DNA diploid range. On follow-up, five children are alive and well 2 to 7 years after treatment. Three children died of tumor progression with metastases to lymph nodes and lungs. One child had been diagnosed only recently, and in one the disease has run a protractive course with multiple recurrences. The behavior of these epithelioid sarcomas in children is similar to that seen in adults, the prognosis being dependent on radical tumor surgery preventing recurrent disease. Long-term follow-up is necessary because the tumor may recur many years after the primary tumor was removed.
上皮样肉瘤是一种罕见肿瘤,大多数病例发生于年轻人,儿童期罕见。我们已获取11例该疾病患者的数据及组织学材料。3例患者的原发部位在头颈部,1例在腹股沟区,7例在四肢。患者年龄范围为12周龄至13岁。男性多于女性,比例为1.75。肿瘤呈现典型的结节状坏死模式。3例可见巨大破骨细胞样细胞。免疫组化和电镜检查结果与既往上皮样肉瘤的观察结果一致。1例光镜下可见小的深色细胞岛,电镜下其周围有基膜。巢内细胞未分化。6例经流式细胞术研究的肿瘤处于DNA二倍体范围。随访中,5例儿童在治疗后2至7年存活且状况良好。3例儿童因肿瘤进展并转移至淋巴结和肺部而死亡。1例儿童最近才被诊断,1例病情呈迁延性,多次复发。儿童这些上皮样肉瘤的行为与成人相似,预后取决于根治性肿瘤手术以防止疾病复发。由于肿瘤可能在原发肿瘤切除多年后复发,因此需要长期随访。