Calder V L, Domigan N M, George P M, Donaldson I M, Winterbourn C C
Department of Pathology, Christchurch School of Medicine, New Zealand.
Neurosci Lett. 1995 Apr 21;189(3):143-6. doi: 10.1016/0304-3940(95)11476-d.
Superoxide dismutase glu100-->gly, a mutation known to be associated with familial motor neuron disease (familial amyotrophic lateral sclerosis) has been detected in one symptomatic and five of seven asymptomatic members of a family with a history of this disease. On average, the individuals with the mutation had 75% of normal red blood cell superoxide dismutase activity. Native polyacrylamide gels stained for superoxide dismutase activity showed two abnormal bands in the family members identified as carrying the mutation. This indicates that active mutant enzyme is present in red cells and forms stable homodimers and heterodimers with the normal chain. A silent mutation in exon 4, not associated with motor neuron disease, was also detected in one family member.
已在一个有家族性运动神经元病(家族性肌萎缩侧索硬化症)病史的家族中,在一名有症状成员和七名无症状成员中的五名中检测到超氧化物歧化酶谷氨酸100突变为甘氨酸,该突变已知与家族性运动神经元病相关。平均而言,携带该突变的个体红细胞超氧化物歧化酶活性为正常水平的75%。用超氧化物歧化酶活性染色的天然聚丙烯酰胺凝胶在被鉴定为携带该突变的家族成员中显示出两条异常条带。这表明红细胞中存在有活性的突变酶,并与正常链形成稳定的同型二聚体和异型二聚体。在一名家族成员中还检测到外显子4中的一个沉默突变,该突变与运动神经元病无关。