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Identification of mutations in the Wiskott-Aldrich syndrome gene and characterization of a polymorphic dinucleotide repeat at DXS6940, adjacent to the disease gene.

作者信息

Kwan S P, Hagemann T L, Radtke B E, Blaese R M, Rosen F S

机构信息

Department of Immunology, Rush Medical School, Chicago, IL 60612, USA.

出版信息

Proc Natl Acad Sci U S A. 1995 May 9;92(10):4706-10. doi: 10.1073/pnas.92.10.4706.

DOI:10.1073/pnas.92.10.4706
PMID:7753869
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC42013/
Abstract

The Wiskott-Aldrich syndrome (WAS) is an X-chromosome-linked recessive disease characterized by eczema, thrombocytopenia, and immunodeficiency. The disease gene has been localized to the proximal short arm of the X chromosome and recently isolated through positional cloning. The function of the encoded protein remains undetermined. In this study we have characterized mutations in 12 unrelated patients to confirm the identity of the disease gene. We have also revised the coding sequence and genomic structure for the WAS gene. To analyze further the transmittance of the disease gene, we have characterized a polymorphic microsatellite at the DXS6940 locus within 30 kb of the gene and demonstrate the inheritance of the affected alleles in families with a history of WAS.

摘要
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/16da/42013/6586a06a4963/pnas01486-0645-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/16da/42013/a45b6bf7c554/pnas01486-0644-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/16da/42013/6586a06a4963/pnas01486-0645-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/16da/42013/a45b6bf7c554/pnas01486-0644-a.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/16da/42013/6586a06a4963/pnas01486-0645-a.jpg

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1
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Proc Natl Acad Sci U S A. 1995 May 9;92(10):4706-10. doi: 10.1073/pnas.92.10.4706.
2
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5
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