Dietz H C, Kendzior R J
Department of Pediatrics, Johns Hopkins University School of Medicine, Baltimore, Maryland 21205.
Nat Genet. 1994 Oct;8(2):183-8. doi: 10.1038/ng1094-183.
Although nonsense mutations have been associated with the skipping of specific constitutively spliced exons in selected genes, notably the fibrillin gene, the basis for this association is unclear. Now, using chimaeric constructs in a model in vivo expression system, premature termination codons are identified as determinants of splice site selection. Nonsense codon recognition prior to RNA splicing necessitates the ability to read the frame of precursor mRNA in the nucleus. We propose that maintenance of an open reading frame can serve as an additional level of scrutiny during exon definition. This process may have pathogenic and evolutionary significance.
尽管无义突变已与特定基因(尤其是原纤蛋白基因)中组成型剪接外显子的跳跃相关联,但这种关联的基础尚不清楚。现在,利用体内表达系统模型中的嵌合构建体,提前终止密码子被确定为剪接位点选择的决定因素。RNA剪接之前对无义密码子的识别需要在细胞核中读取前体mRNA框架的能力。我们提出,开放阅读框的维持可作为外显子定义过程中额外的审查水平。这一过程可能具有致病和进化意义。