Barr F G, Galili N, Holick J, Biegel J A, Rovera G, Emanuel B S
Division of Human Genetics and Molecular Biology, Children's Hospital of Philadelphia, Pennsylvania.
Nat Genet. 1993 Feb;3(2):113-7. doi: 10.1038/ng0293-113.
We have determined that PAX3 (found previously to be mutated in Waardenburg syndrome) is the chromosome 2 locus rearranged by the t(2;13)(q35;q14) translocation of the paediatric solid tumour alveolar rhabdomyosarcoma. The rearrangement breakpoints occur within an intron downstream of the paired box and homeodomain-encoding regions. Upstream PAX3 sequences hybridize to a novel transcript in t(2;13)-containing lines. Cloning and characterization of this novel transcript indicate that the translocation juxtaposes the PAX3 DNA binding elements with chromosome 13 sequences, suggesting formation of a hybrid transcription factor. Therefore, PAX3 gene alterations are associated with two completely unrelated human diseases.
我们已经确定,PAX3(先前发现其在瓦登伯格综合征中发生突变)是小儿实体瘤肺泡横纹肌肉瘤的t(2;13)(q35;q14)易位所重排的2号染色体位点。重排断点出现在配对盒和同源结构域编码区域下游的一个内含子内。上游PAX3序列与含t(2;13)的细胞系中的一种新转录本杂交。对这种新转录本的克隆和特性分析表明,该易位使PAX3 DNA结合元件与13号染色体序列并列,提示形成了一种杂交转录因子。因此,PAX3基因改变与两种完全不相关的人类疾病有关。