Hahn A F
Department of Clinical Neurological Sciences, University of Western Ontario, London, Canada.
Brain Pathol. 1993 Apr;3(2):147-55. doi: 10.1111/j.1750-3639.1993.tb00739.x.
The neuronal forms of hereditary motor and sensory neuropathy (HMSN) are genetically heterogeneous with observed autosomal dominant, autosomal recessive and X-linked dominant inheritance. All three forms are characterized by degeneration of select populations of motor and sensory neurons with accompanying atrophy and degeneration of their axons. Large calibre myelinated fibres are predominantly affected and fibre degeneration and fibre loss progresses from distally to proximally. Attempts of regeneration are noted in all except the severe childhood form. The clinical picture is that of peroneal and distal leg muscle wasting and weakness, distal sensory loss and areflexia. Hand muscles may be severely affected in the autosomal recessive and X-linked dominant forms. Motor and sensory nerve conduction velocities are only moderately slowed and evoked maximum compound motor and sensory amplitudes are reduced according to the degree of fibre loss. The gene locus remains unknown in both the autosomal dominant and autosomal recessive types. For the X-linked dominant HMSN, the gene locus has been mapped closely by linkage analysis to DNA loci in the pericentromeric region of the X-chromosome.
遗传性运动和感觉神经病(HMSN)的神经元形式在遗传上具有异质性,观察到常染色体显性、常染色体隐性和X连锁显性遗传。所有这三种形式的特征是特定运动和感觉神经元群体的退化,以及其轴突随之而来的萎缩和退化。大口径有髓纤维主要受到影响,纤维退化和纤维丧失从远端向近端发展。除严重的儿童形式外,在所有病例中均可见再生尝试。临床表现为腓骨肌和小腿远端肌肉萎缩和无力、远端感觉丧失和反射消失。常染色体隐性和X连锁显性形式中手部肌肉可能受到严重影响。运动和感觉神经传导速度仅适度减慢,诱发的最大复合运动和感觉振幅根据纤维丧失程度而降低。常染色体显性和常染色体隐性类型的基因位点均未知。对于X连锁显性HMSN,通过连锁分析已将基因位点紧密定位到X染色体着丝粒周围区域的DNA位点。