Magaudda A, Dalla Bernardina B, De Marco P, Sfaello Z, Longo M, Colamaria V, Daniele O, Tortorella G, Tata M A, Di Perri R
Institute of Neurological and Neurosurgical Sciences, University of Messina, Italy.
J Neurol Neurosurg Psychiatry. 1993 Aug;56(8):885-9. doi: 10.1136/jnnp.56.8.885.
Twenty patients affected by bilateral occipital cortical-subcortical calcification (BOC) are described, 19 (95%) had epilepsy. In 8 of 16 cases studied, intestinal biopsy revealed coeliac disease. Fourteen patients had occipital partial epilepsy with a relatively benign outcome, while 4 patients were affected by a severe form of epilepsy, with very frequent, drug-resistant, generalised and partial seizures with mental deterioration. One patient had a single episode of convulsive status epilepticus at four months of age. The neurological examination was normal in all patients. CT showed flocculo-nodular, cortico-subcortical BOC, without enhancement and without lobar or hemispheric atrophy. MRI was normal. The clinical and neuroimaging features of these patients are different therefore from those with the Sturge-Weber Syndrome. The study confirms a high prevalence of coliac disease in patients with BOC, but the relationship between these two pathologies still needs to be clarified.
本文描述了20例双侧枕叶皮质 - 皮质下钙化(BOC)患者,其中19例(95%)患有癫痫。在研究的16例患者中,8例经肠道活检发现患有乳糜泻。14例患者患有枕叶部分性癫痫,预后相对良好,而4例患者患有严重形式的癫痫,发作频繁、耐药,有全身性和部分性发作,并伴有精神衰退。1例患者在4个月大时发生了一次惊厥性癫痫持续状态。所有患者的神经系统检查均正常。CT显示为絮状结节状、皮质 - 皮质下BOC,无强化,无叶或半球萎缩。MRI正常。因此,这些患者的临床和神经影像学特征与斯特奇 - 韦伯综合征患者不同。该研究证实BOC患者中乳糜泻的患病率很高,但这两种疾病之间的关系仍有待阐明。