Bartram C, Edwards R H, Clague J, Beynon R J
Department of Biochemistry, University of Liverpool, UK.
Hum Mol Genet. 1993 Aug;2(8):1291-3. doi: 10.1093/hmg/2.8.1291.
McArdle's disease is an inherited disease that results from a lack of functional muscle glycogen phosphorylase. We report here the identification of a C to T transition in exon 1 of the muscle phosphorylase gene found in all patients studied. This base pair mutation results in the substitution of a stop codon (TGA) for the codon (CGA) for Arg49 in the mature protein, and generates a novel restriction site for NlaIII. Of sixteen McArdle's patients, ten are homozygous for this mutation; the remainder are heterozygous. Additional unidentified mutations must lead to the McArdle's phenotype in the latter group of patients.
麦克尔氏病是一种由于缺乏功能性肌肉糖原磷酸化酶而导致的遗传性疾病。我们在此报告,在所研究的所有患者中均发现肌肉磷酸化酶基因外显子1中存在一个从C到T的转换。这个碱基对突变导致成熟蛋白中第49位精氨酸的密码子(CGA)被终止密码子(TGA)取代,并产生了一个新的NlaIII酶切位点。在16例麦克尔氏病患者中,10例为该突变的纯合子;其余为杂合子。在后者这组患者中,必定存在其他未确定的突变导致了麦克尔氏病的表型。