Bech-Hansen N T, Pearce W G
Molecular Genetics Unit, Alberta Children's Hospital, University of Calgary, Canada.
Ophthalmic Genet. 1995 Sep;16(3):113-8. doi: 10.3109/13816819509059970.
The identification by fundus examination of those females carrying an X-linked retinitis pigmentosa (RP) gene can reportedly be as high as 87%. In genetic counselling sessions with young females with a 50% risk of being a carrier who wished to know their status, it has not been possible to achieve such a level of success. A review and reanalysis of previous reports indicated that if a tapetal-like reflex was not present in those age 35 years or less, the likelihood of identifying a carrier by fundus examination was small. A family with 7 females with a 50% risk of being a carrier of X-linked RP was evaluated using haplotype analysis in an attempt to identify the X chromosome carrying the RP gene. In the family described, it was possible to establish that a mutation in the RP3 locus most likely causes the disease. This has permitted the determination of the carrier status in each of the females with a high degree of certainty.
据报道,通过眼底检查识别携带X连锁视网膜色素变性(RP)基因的女性,成功率可高达87%。在对有50%携带风险且希望了解自身状况的年轻女性进行遗传咨询时,尚未能达到如此高的成功率。对既往报告的回顾与重新分析表明,如果35岁及以下人群不存在类毯样反光,通过眼底检查识别携带者的可能性较小。对一个有7名女性、携带X连锁RP基因风险为50%的家系进行单倍型分析,以试图确定携带RP基因的X染色体。在所描述的这个家系中,有可能确定RP3位点的突变很可能导致了该疾病。这使得能够高度准确地确定每名女性的携带者状态。