Leube B, Rudnicki D, Ratzlaff T, Kessler K R, Benecke R, Auburger G
Department of Neurology, University Hospital, Düsseldorf, Germany.
Hum Mol Genet. 1996 Oct;5(10):1673-7. doi: 10.1093/hmg/5.10.1673.
Idiopathic torsion dystonia (ITD) is a group of movement disorders which is usually inherited in an autosomal dominant manner with reduced penetrance. Most patients with ITD present with focal dystonia at adult age. However, thus far, this common subform remained unmapped chromosomally. In contrast, a rare early onset, more generalized form of ITD has been mapped to chromosome 9q34. Our linkage study in a large pedigree with seven definitely affected, six possibly affected and 16 phenotypically unaffected family members assigns an ITD gene for the common focal form with a maximal lod score of 3.17 to the region telomeric of D18S1153 on chromosome 18p.
特发性扭转性肌张力障碍(ITD)是一组运动障碍疾病,通常以常染色体显性方式遗传,外显率降低。大多数ITD患者在成年时出现局灶性肌张力障碍。然而,迄今为止,这种常见的亚型在染色体上仍未定位。相比之下,一种罕见的早发性、更广泛形式的ITD已被定位到9号染色体q34区域。我们在一个大型家系中进行的连锁研究,该家系中有7名明确患病、6名可能患病和16名表型正常的家庭成员,将常见局灶性形式的ITD基因定位到18号染色体p臂上D18S1153端粒区域,最大对数优势得分为3.17。