Lo Ten Foe J R, Rooimans M A, Bosnoyan-Collins L, Alon N, Wijker M, Parker L, Lightfoot J, Carreau M, Callen D F, Savoia A, Cheng N C, van Berkel C G, Strunk M H, Gille J J, Pals G, Kruyt F A, Pronk J C, Arwert F, Buchwald M, Joenje H
Department of Human Genetics, Free University, Amsterdam, The Netherlands.
Nat Genet. 1996 Nov;14(3):320-3. doi: 10.1038/ng1196-320.
Fanconi anaemia (FA) is an autosomal recessive disorder characterized by a diversity of clinical symptoms including skeletal abnormalities, progressive bone marrow failure and a marked predisposition to cancer. FA cells exhibit chromosomal instability and hyper-responsiveness to the clastogenic and cytotoxic effects of bifunctional alkylating (cross-linking) agents, such as diepoxybutane (DEB) and mitomycin C (MMC). Five complementation groups (A-E) have been distinguished on the basis of somatic cell hybridization experiments, with group FA-A accounting for over 65% of the cases analysed. A cDNA for the group C gene (FAC) was reported and localized to chromosome 9q22.3 (ref.8). Genetic map positions were recently reported for two more FA genes, FAA (16q24.3) and FAD (3p22-26). Here we report the isolation of a cDNA representing the FAA gene, following an expression cloning method similar to the one used to clone the FAC gene. The 5.5-kb cDNA has an open reading frame of 4,368 nucleotides. In contrast to the 63-kD cytosolic protein encoded by the FAC gene, the predicted FAA protein (M(r) 162, 752) contains two overlapping bipartite nuclear localization signals and a partial leucine zipper consensus, which are suggestive of a nuclear localization.
范可尼贫血(FA)是一种常染色体隐性疾病,其特征为多种临床症状,包括骨骼异常、进行性骨髓衰竭以及显著的癌症易感性。FA细胞表现出染色体不稳定以及对双功能烷化(交联)剂(如二环氧丁烷(DEB)和丝裂霉素C(MMC))的致断裂和细胞毒性作用具有高反应性。基于体细胞杂交实验已区分出五个互补组(A - E),其中FA - A组占所分析病例的65%以上。已报道了C组基因(FAC)的cDNA,并将其定位到9号染色体q22.3区域(参考文献8)。最近又报道了另外两个FA基因FAA(16q24.3)和FAD(3p22 - 26)的遗传图谱位置。在此,我们报告了通过与用于克隆FAC基因相似的表达克隆方法分离出一个代表FAA基因的cDNA。该5.5kb的cDNA具有一个4368个核苷酸的开放阅读框。与FAC基因编码的63kD胞质蛋白不同,预测的FAA蛋白(分子量162,752)包含两个重叠的双分型核定位信号和一个部分亮氨酸拉链共有序列,提示其定位于细胞核。