Wanders R J, Dekker C, Ofman R, Schutgens R B, Mooijer P
University Hospital Amsterdam, Department of Pediatrics, The Netherlands.
J Inherit Metab Dis. 1995;18 Suppl 1:101-12. doi: 10.1007/BF00711433.
Identification of a patient as suffering from a peroxisomal disorder usually starts by the finding of elevated very long-chain fatty acids in plasma and/or serum. This is followed by more detailed studies in blood, fibroblasts and tissues, including immunoblot analysis. Indeed, immunoblot analysis has become a valuable tool in the correct diagnosis and assignment of individual patients, except for X-linked adrenoleukodystrophy (X-ALD). We describe a simple immunoblotting procedure applicable to liver and fibroblast homo-genates using antibodies raised against catalase and the three beta-oxidation enzyme proteins acyl-CoA oxidase I, bifunctional protein and peroxisomal thiolase. The same procedure can also be used for chorionic villus biopsy specimens and has now become the method of choice for the prenatal diagnosis of Zellweger syndrome (and other disorders of peroxisome biogenesis) and rhizomelic chondrodysplasia punctata.
确定患者患有过氧化物酶体疾病通常始于发现血浆和/或血清中极长链脂肪酸水平升高。随后会在血液、成纤维细胞和组织中进行更详细的研究,包括免疫印迹分析。实际上,免疫印迹分析已成为正确诊断和区分个体患者的重要工具,但X连锁肾上腺脑白质营养不良(X-ALD)除外。我们描述了一种简单的免疫印迹程序,该程序适用于肝脏和成纤维细胞匀浆,使用针对过氧化氢酶以及三种β氧化酶蛋白(酰基辅酶A氧化酶I、双功能蛋白和过氧化物酶体硫解酶)产生的抗体。相同的程序也可用于绒毛膜绒毛活检标本,现已成为泽尔韦格综合征(以及其他过氧化物酶体生物发生障碍)和点状软骨发育不良产前诊断的首选方法。