McDonnell G V, Hawkins S A
Northern Ireland Neurology Service, Royal Victoria Hospital, Belfast, UK.
J Neurol Neurosurg Psychiatry. 1998 Apr;64(4):451-4. doi: 10.1136/jnnp.64.4.451.
To investigate the clinical and demographic characteristics of primary progressive multiple sclerosis (PPMS) in Northern Ireland and to establish a database of such patients for genetic and immunological studies and future therapeutic trials.
Diagnosis and categorisation were performed by two neurologists, potential cases being identified from the following sources: neurology outpatient clinics; neurology inpatients; a review of hospital discharges; and an ongoing epidemiological study of multiple sclerosis in Northern Ireland. Only those with a progressive course from onset and a clear history of no prior relapses were accepted. Potential cases were invited for interview and assessment, the minimal record of disability (MRD) being established.
One hundred and eleven cases of PPMS have been identified, 63 women and 48 men (ratio 1.3:1), with a mean age at onset of 39.5 (SD 11.0) (range 17-66)years, and mean disease duration of 13.6 (SD 9.3)years. The mean interval between onset and diagnosis was 4.7 (SD 4.2) years. Nineteen patients (17.1%) did not satisfy the requirements for any category in the Poser criteria. Motor disturbance was the commonest mode of onset (67.6%) with visual loss occurring only rarely at onset (3.6%). Kurtzke EDSS scores were concentrated at the upper end of the scale with a median of 6.0 and levels of unemployment and financial dependence were high.
PPMS in Northern Ireland has a generally later age at onset, lower female preponderance, and predominantly motor onset compared with other subgroups of multiple sclerosis. The delay to diagnosis reflects the often insidious onset and the nature of the clinical course makes application of the Poser criteria difficult. Levels of neurological impairment, disability, and handicap as measured by the MRD are high.
调查北爱尔兰原发性进行性多发性硬化症(PPMS)的临床和人口统计学特征,并建立此类患者的数据库,用于基因和免疫学研究以及未来的治疗试验。
由两名神经科医生进行诊断和分类,从以下来源识别潜在病例:神经科门诊;神经科住院患者;医院出院记录审查;以及北爱尔兰正在进行的多发性硬化症流行病学研究。仅接受那些自发病起病程呈进行性且无既往复发明确病史的患者。邀请潜在病例进行访谈和评估,建立最小残疾记录(MRD)。
已识别出111例PPMS患者,其中63例女性和48例男性(比例为1.3:1),发病时的平均年龄为39.5岁(标准差11.0)(范围17 - 66岁),平均病程为13.6年(标准差9.3)。发病至诊断的平均间隔时间为4.7年(标准差4.2)。19名患者(17.1%)不符合波泽标准中任何类别的要求。运动障碍是最常见的起病方式(67.6%),发病时仅有极少数患者出现视力丧失(3.6%)。库尔特克扩展残疾状态量表(EDSS)评分集中在量表的较高端,中位数为6.0,失业和经济依赖水平较高。
与多发性硬化症的其他亚组相比,北爱尔兰的PPMS发病年龄通常较晚,女性优势较低,且主要以运动起病。诊断延迟反映了起病往往隐匿,临床病程的性质使得应用波泽标准困难。通过MRD测量的神经功能损害、残疾和障碍水平较高。