Falini B, Bigerna B, Fizzotti M, Pulford K, Pileri S A, Delsol G, Carbone A, Paulli M, Magrini U, Menestrina F, Giardini R, Pilotti S, Mezzelani A, Ugolini B, Billi M, Pucciarini A, Pacini R, Pelicci P G, Flenghi L
Institute of Hematology, University of Perugia, Italy.
Am J Pathol. 1998 Sep;153(3):875-86. doi: 10.1016/S0002-9440(10)65629-5.
The t(2;5)(p23;q35) translocation associated with CD30-positive anaplastic large cell lymphoma results in the production of a NPM-ALK chimeric protein, consisting of the N-terminal portion of the NPM protein joined to the entire cytoplasmic domain of the neural receptor tyrosine kinase ALK. The ALK gene products were identified in paraffm sections by using a new anti-ALK (cytoplasmic portion) monoclonal antibody (ALKc) that tends to react more strongly than a previously described ALK1 antibody with the nuclei of ALK-expressing tumor cells after microwave heating in 1 mmol/L ethylenediaminetetraacetic acid buffer, pH 8.0. The ALKc monoclonal antibody reacted selectively with 60% of anaplastic large cell lymphoma cases (60 of 100), which occurred mainly in the first three decades of life and consistently displayed a T/null phenotype. This group of ALK-positive tumors showed a wide morphological spectrum including cases with features of anaplastic large cell lymphoma "common" type (75%), "lymphohistiocytic" (10%), "small cell" (8.3%), "giant cell" (3.3%), and "Hodgkin's like" (3.3%). CD30-positive large anaplastic cells expressing the ALK protein both in the cytoplasm and nucleus represented the dominant tumor population in the common, Hodgkin's-like and giant cell types, but they were present at a smaller percentage (often with a perivascular distribution) also in cases with lymphohistiocytic and small cell features. In this study, the ALKc antibody also allowed us to identify small neoplastic cells (usually CD30 negative) with nucleus-restricted ALK positivity that were, by definition, more evident in the small cell variant but were also found in cases with lymphohistiocytic, common, and "Hodgkin's-like" features. These findings, which have not been previously emphasized, strongly suggest that the neoplastic lesion (the NPM-ALK gene) must be present both in the large anaplastic and small tumor cells, and that ALK-positive lymphomas lie on a spectrum, their position being defined by the ratio of small to large neoplastic cells. Notably, about 15% of all ALK-positive lymphomas (usually of the common or giant cell variant) showed a cytoplasm-restricted ALK positivity, which suggests that the ALK gene may have fused with a partner(s) other than NPM. From a diagnostic point of view, detection of the ALK protein was useful in distinguishing anaplastic large cell lymphoma cases of lymphohistiocytic and small cell variants from reactive conditions and other peripheral T-cell lymphoma subtypes, as well as for detecting a small number of tumor cells in lymphohemopoietic tissues. In conclusion, ALK positivity appears to define a clinicopathological entity with a T/null phenotype ("ALK lymphomas"), but one that shows a wider spectrum of morphological patterns than has been appreciated in the past.
与CD30阳性间变性大细胞淋巴瘤相关的t(2;5)(p23;q35)易位导致产生一种NPM-ALK嵌合蛋白,该蛋白由NPM蛋白的N端部分与神经受体酪氨酸激酶ALK的整个胞质结构域连接而成。通过使用一种新的抗ALK(胞质部分)单克隆抗体(ALKc)在石蜡切片中鉴定ALK基因产物,在pH 8.0的1 mmol/L乙二胺四乙酸缓冲液中微波加热后,该抗体与表达ALK的肿瘤细胞核的反应往往比先前描述的ALK1抗体更强。ALKc单克隆抗体选择性地与60%的间变性大细胞淋巴瘤病例(100例中的60例)反应,这些病例主要发生在生命的前三十年,并且始终表现为T/null表型。这组ALK阳性肿瘤表现出广泛的形态学谱,包括具有间变性大细胞淋巴瘤“常见”型(75%)、“淋巴组织细胞型”(10%)、“小细胞型”(8.3%)、“巨细胞型”(3.3%)和“霍奇金样”(3.3%)特征的病例。在常见型、霍奇金样型和巨细胞型中,表达ALK蛋白的CD30阳性大间变性细胞代表主要的肿瘤细胞群,但在具有淋巴组织细胞和小细胞特征的病例中也以较小的百分比存在(通常呈血管周围分布)。在本研究中,ALKc抗体还使我们能够识别核限制性ALK阳性的小肿瘤细胞(通常CD30阴性),根据定义,这些细胞在小细胞变体中更明显,但在具有淋巴组织细胞、常见和“霍奇金样”特征的病例中也能发现。这些以前未被强调的发现强烈表明,肿瘤性病变(NPM-ALK基因)必须同时存在于大间变性细胞和小肿瘤细胞中,并且ALK阳性淋巴瘤处于一个谱系中,其位置由小肿瘤细胞与大肿瘤细胞的比例决定。值得注意的是,所有ALK阳性淋巴瘤中约15%(通常为常见型或巨细胞变体)表现为胞质限制性ALK阳性,这表明ALK基因可能与NPM以外的其他伙伴融合。从诊断的角度来看,ALK蛋白的检测有助于将淋巴组织细胞型和小细胞变体的间变性大细胞淋巴瘤病例与反应性情况及其他外周T细胞淋巴瘤亚型区分开来,也有助于检测淋巴造血组织中的少量肿瘤细胞。总之,ALK阳性似乎定义了一种具有T/null表型的临床病理实体(“ALK淋巴瘤”),但它表现出比过去认识到的更广泛的形态学模式谱。