Mullaney P B, Parsons M A, Weatherhead R G, Karcioglu Z A
King Khaled Eye Specialist Hospital, Riyadh, Saudi Arabia.
Eye (Lond). 1998;12 ( Pt 3a):353-7. doi: 10.1038/eye.1998.85.
Evaluation of 4-month-old girl who presented with congenital cataracts revealed heterochromia iridis, fundus hypopigmentation, residual white forelock and sensory neural hearing loss--findings consistent with Waardenburg syndrome type II. Bilateral peripheral iridectomies performed at lensectomy provided tissue for evaluation. Light microscopy revealed fewer melanocytes in the blue iris than in the brown. Electron microscopic examination showed a significant (p = 0.0001) reduction in melanosome size in the blue iris, and the nerve endings contained fewer vesicles. A defect in neural crest cell migration and melanin synthesis may be responsible for the heterochromia iridis seen in Waardenburg syndrome type II.
对一名患有先天性白内障的4个月大女童进行评估时发现虹膜异色、眼底色素减退、残留白色额发和感音神经性听力损失——这些发现与II型瓦登伯革氏综合征相符。在晶状体切除术中进行的双侧周边虹膜切除术提供了用于评估的组织。光学显微镜检查显示,蓝色虹膜中的黑素细胞比棕色虹膜中的少。电子显微镜检查显示,蓝色虹膜中的黑素体大小显著减小(p = 0.0001),且神经末梢含有的囊泡较少。神经嵴细胞迁移和黑色素合成缺陷可能是II型瓦登伯革氏综合征中所见虹膜异色的原因。