Martínez Ferro M, Milner R, Voto L, Zapaterio J, Cannizzaro C, Rodríguez S, Bonifacino G, Sanchez J M, Adzick N S
Department of Pediatric Surgery and Neonatal Intensive Care Unit, National Pediatric Hospital 'J.P.Garrahan', Universidad de Buenos Aires,
Fetal Diagn Ther. 1998 Nov-Dec;13(6):343-7. doi: 10.1159/000020866.
Alimentary tract duplication cysts are rarely diagnosed in utero. We report two fetal patients that presented with intrathoracic alimentary tract duplication cysts, mediastinal shift and hydrops. In one fetus, the cyst continued into the fetal abdomen and pelvis through a left diaphragmatic hernia. Despite successful ultrasound-guided needle aspirations in both fetuses, there was rapid reaccumulation of the fluid and recurrence of the mediastinal shift, prompting the placement of a thoracoamniotic shunt. In one fetus, there was rapid resolution of the mediastinal shift with the disappearance of the hydrops within 2 weeks. The second fetus suffered an intrauterine demise 2 days after the shunt placement. Postnatal resection in the surviving infant revealed a large cyst consistent with an intrathoracic duplication of the stomach. The autopsy of the second fetus revealed an intrathoracic duplication cyst of the stomach and proximal small intestine.
消化道重复囊肿在子宫内很少被诊断出来。我们报告了两名患有胸腔内消化道重复囊肿、纵隔移位和水肿的胎儿患者。在一名胎儿中,囊肿通过左侧膈疝延伸至胎儿腹部和骨盆。尽管对两名胎儿均成功进行了超声引导下的针吸术,但液体迅速重新积聚,纵隔移位复发,促使放置了胸羊膜分流管。在一名胎儿中,纵隔移位在2周内迅速消退,水肿消失。第二名胎儿在分流管放置后2天宫内死亡。存活婴儿的产后切除显示一个与胃的胸腔内重复一致的大囊肿。第二名胎儿的尸检显示胃和近端小肠的胸腔内重复囊肿。