Luppis B, Ventruto V
Acta Haematol. 1979;61(4):216-21. doi: 10.1159/000207659.
Globin chain synthesis has been investigated for the first time in 2 patients homozygous for haemoglobin Lepore, although the 2 brothers have the same haemoglobin genotype the severity of the diseases is very different. The purpose of this study was to try and find out the reason for the different severity in the clinical manifestations. In the 2 patients a different excess of alpha-chain synthesis was observed, the higher excess being present in the subject carrying the more severe anaemia. This result strongly suggests that in homozygous haemoglobin Lepore disease, as in beta-thalassaemia, the degree of globin chain imbalance is responsible for the clinical manifestations.
首次对2名血红蛋白Lepore纯合子患者的珠蛋白链合成进行了研究,尽管这2名兄弟具有相同的血红蛋白基因型,但疾病的严重程度却大不相同。本研究的目的是试图找出临床表现严重程度不同的原因。在这2名患者中,观察到α链合成存在不同程度的过量,贫血更严重的患者中α链过量程度更高。这一结果有力地表明,在血红蛋白Lepore病纯合子中,与β地中海贫血一样,珠蛋白链失衡的程度决定了临床表现。