Kerr B, Smith V, Patel R, Ladusans E, Sillence D O
Department of Genetics, Royal Manchester Children's Hospital, UK.
Clin Dysmorphol. 2000 Jul;9(3):167-72. doi: 10.1097/00019605-200009030-00003.
Spondylometaphyseal dysplasia of the Sedaghatian type is a rare dysplasia, characterized by mild limb shortening, but lethal in the neonatal period. We describe three affected male siblings, the offspring of consanguineous parents. One was stillborn. Neonatal death was due to cardiac arrhythmia in two of the siblings. This report confirms the importance of cardiac pathology in this probably autosomal recessive disorder. This diagnosis should be excluded in any newborn with an arrhythmia as the clinical limb shortening may not be obvious.
塞达加蒂安型脊椎干骺端发育不良是一种罕见的发育不良,其特征为肢体轻度缩短,但在新生儿期具有致死性。我们描述了三名患病男性同胞,他们是近亲父母的后代。其中一名为死产。另外两名同胞因心律失常在新生儿期死亡。本报告证实了心脏病理学在这种可能为常染色体隐性遗传疾病中的重要性。对于任何有心律失常的新生儿均应排除该诊断,因为临床可见的肢体缩短可能并不明显。