Wilken J J, Meier F A, Kornstein M J
Department of Pathology, Medical College of Virginia, Virginia Commonwealth University, Richmond, VA 23298-0662, USA.
Arch Pathol Lab Med. 2000 Oct;124(10):1542-4. doi: 10.5858/2000-124-1542-KHOTT.
Kaposiform hemangioendothelioma is a rare pediatric neoplasm that presents most commonly in the soft tissues. We report the case of a 1-month-old infant who presented with stridor and was found to have a diffusely infiltrating tumor in the thymus that extended into the pericardium and up the carotid sheaths. Histologic examination revealed a vascular tumor infiltrating among the lobules of the lymphocyte-depleted thymus. The lesion had features of both a capillary hemangioma and Kaposi sarcoma. Immunoperoxidase studies on formalin-fixed, paraffin-embedded tissue demonstrated the neoplastic endothelial cells to be positive for vascular markers CD31 and CD34. Antibody to factor VIII-related antigen labeled feeding vessels, but failed to stain the lobules of tumor. Although these tumors have been treated in a fashion similar to capillary hemangiomas in the past, it may be important to differentiate Kaposiform hemangioendotheliomas because of their association with Kasabach-Merritt syndrome and recent success with more aggressive chemotherapy regimens.
卡波西型血管内皮瘤是一种罕见的儿科肿瘤,最常见于软组织。我们报告了一例1个月大的婴儿,该婴儿出现喘鸣,经检查发现胸腺有弥漫性浸润性肿瘤,肿瘤延伸至心包并向上累及颈动脉鞘。组织学检查显示,血管性肿瘤浸润于淋巴细胞减少的胸腺小叶之间。该病变具有毛细血管瘤和卡波西肉瘤的特征。对福尔马林固定、石蜡包埋组织进行的免疫过氧化物酶研究表明,肿瘤性内皮细胞对血管标记物CD31和CD34呈阳性。抗VIII因子相关抗原抗体标记了供血血管,但未能对肿瘤小叶进行染色。尽管过去这些肿瘤的治疗方式与毛细血管瘤相似,但由于卡波西型血管内皮瘤与卡萨巴赫-梅里特综合征相关,且最近采用更积极的化疗方案取得了成功,因此区分它们可能很重要。