Snodgrass P J, DeLong G R
N Engl J Med. 1976 Apr 15;294(16):855-60. doi: 10.1056/NEJM197604152941601.
Assay of urea-cycle enzymes in liver tissue showed ornithine transcarbamylase activities of 18 to 72 per cent of the normal mean in eight patients with Reye's syndrome, below the range of normal in seven of eight, and, in six cases, as low as those in females with X-linked deficiency of this enzyme. Carbamyl phosphate synthetase activities were less than 32 per cent of controls in two patients. Argininosuccinate synthetase and lyase activities were normal in seven patients. Arginase was normal in two biopsy specimens, but below normal in four of five autopsy specimens. The Km's for ornithine and carbamyl phosphate, pH optimum, and heat lability of ornithine transcarbamylase were normal. Two patients excreted 0.64 and 0.58 g per kilogram per day of urinary nitrogen at the peak of hyperammonemia, in spite of peritoneal dialysis. The hyperammonemia of Reye's syndrome apparently results from excess waste nitrogen that overwhelms the ability of reduced ornithine transcarbamylase (and occasionally carbamyl phosphate synthetase) to detoxify the ammonia load.
对肝脏组织中的尿素循环酶进行检测发现,8例瑞氏综合征患者的鸟氨酸转氨甲酰酶活性为正常均值的18%至72%,8例中有7例低于正常范围,在6例中,其活性低至患有该酶X连锁缺陷的女性患者的水平。2例患者的氨甲酰磷酸合成酶活性低于对照组的32%。7例患者的精氨琥珀酸合成酶和裂解酶活性正常。2例活检标本中的精氨酸酶正常,但5例尸检标本中有4例低于正常水平。鸟氨酸转氨甲酰酶对鸟氨酸和氨甲酰磷酸的米氏常数、最适pH值以及热稳定性均正常。尽管进行了腹膜透析,但2例患者在高氨血症高峰期每天每千克体重排泄0.64克和0.58克尿氮。瑞氏综合征的高氨血症显然是由于过量的代谢废物氮超过了降低的鸟氨酸转氨甲酰酶(偶尔还有氨甲酰磷酸合成酶)对氨负荷进行解毒的能力所致。