Anvret M, Blombäck M, Lindstedt M, Söderlind E, Tapper-Persson M, Thelander A C
Department of Clinical Genetics, Karolinska Hospital, Stockholm, Sweden.
Hum Genet. 1992 May;89(2):147-54. doi: 10.1007/BF00217114.
Twenty-five patients with von Willebrand's disease (vWD) type III were analysed with regard to blood coagulation variables and possible deletions. Nine of the probands and their families were further investigated with DNA linkage analyses. Different patterns of heredity can be suggested in our families with vWD type III, on the basis of blood coagulation analyses. The findings suggest homozygosity in five families and the possibility of compound heterozygosity or a new mutation in the proband in three families. The linkage analyses confirm the results of the coagulation analyses. The segregation of the von Willebrand factor (vWF) gene can be followed in the families, and carrier diagnosis can be made in several of the probands' relatives. The possibility of large deletions in the vWF gene of the probands and their parents was investigated with probes representing the whole vWF cDNA. No deletions were found.
对25例III型血管性血友病(vWD)患者的凝血变量和可能的缺失情况进行了分析。对9名先证者及其家族进一步进行了DNA连锁分析。根据凝血分析结果,在我们的III型vWD家族中可提示不同的遗传模式。研究结果表明,5个家族为纯合子,3个家族中先证者可能为复合杂合子或新发突变。连锁分析证实了凝血分析的结果。在这些家族中可以追踪血管性血友病因子(vWF)基因的分离情况,并且可以对部分先证者的亲属进行携带者诊断。用代表整个vWF cDNA的探针研究了先证者及其父母vWF基因中大片段缺失的可能性。未发现缺失情况。