Hasle H, Jacobsen B B, Asschenfeldt P, Andersen K
Department of Paediatrics, Odense University Hospital, Denmark.
Eur J Pediatr. 1992 Oct;151(10):735-9. doi: 10.1007/BF01959079.
A 14-year-old boy with Klinefelter syndrome (KS) and a large mediastinal tumour is presented. Human chorionic gonadotropin and oestradiol were markedly increased. An attempt at radical resection was performed. Histological examination revealed a malignant germ cell tumour of mixed histologic pattern composed of choriocarcinoma and components of mature teratoma. Four courses of cisplatin, bleomycin, and etoposide were given. The patient is without any evidence of tumour recurrence 20 months after diagnosis. A review of the literature revealed another 40 cases of primary mediastinal germ cell tumour (PMGCT) associated with KS. Compiled data from larger series demonstrate that at least 8% of male patients with PMGCT have KS, 50 times the expected frequency. In contrast to PMGCT in patients without KS, all tumours were of nonseminomatous histology, and the average age was considerably lower, Tumours in prepubertal boys were associated with precocious puberty.
本文报告了一名患有克兰费尔特综合征(KS)并伴有巨大纵隔肿瘤的14岁男孩。人绒毛膜促性腺激素和雌二醇显著升高。尝试进行根治性切除。组织学检查显示为恶性生殖细胞肿瘤,组织学类型混合,由绒毛膜癌和成熟畸胎瘤成分组成。给予了四个疗程的顺铂、博来霉素和依托泊苷。诊断后20个月,患者无任何肿瘤复发迹象。文献回顾发现另外40例与KS相关的原发性纵隔生殖细胞肿瘤(PMGCT)。来自更大系列的汇总数据表明,至少8%的PMGCT男性患者患有KS,是预期频率的50倍。与无KS患者的PMGCT相比,所有肿瘤均为非精原细胞瘤组织学类型,且平均年龄低得多,青春期前男孩的肿瘤与性早熟有关。