Weisstein Jason S, Delgado Eliana, Steinbach Lynne S, Hart Kim, Packman Seymour
Department of Orthopaedic Surgery, University of California, San Francisco, San Francisco, California, USA.
J Pediatr Orthop. 2004 Jan-Feb;24(1):97-101. doi: 10.1097/00004694-200401000-00019.
Bone marrow transplantation (BMT) is effective in ameliorating many of the clinical manifestations of Hurler syndrome. However, long-term data on the natural history of the musculoskeletal disorders of Hurler syndrome after BMT are limited. The authors report the orthopaedic outcomes in seven patients with Hurler syndrome who were successfully engrafted between 1990 and 1999, and have been followed for a mean of 7.6 years since transplantation. Medical records, clinical examinations, and imaging studies were reviewed to assess the development and management of hip dysplasia, genu valgum, spine abnormalities, hand abnormalities, and joint range of motion. BMT does not appear to alter the natural history of the musculoskeletal disorders in Hurler syndrome, although there may be a beneficial effect on upper extremity joint mobility.
骨髓移植(BMT)在改善Hurler综合征的许多临床表现方面是有效的。然而,关于BMT后Hurler综合征肌肉骨骼疾病自然病史的长期数据有限。作者报告了1990年至1999年间成功植入的7例Hurler综合征患者的骨科结局,自移植后平均随访7.6年。回顾了病历、临床检查和影像学研究,以评估髋关节发育不良、膝外翻、脊柱异常、手部异常和关节活动范围的发展及处理情况。骨髓移植似乎并未改变Hurler综合征肌肉骨骼疾病的自然病史,尽管对上肢关节活动度可能有有益影响。