Masterson E L, Murphy P G, O'Meara A, Moore D P, Dowling F E, Fogarty E E
Our Lady's Hospital for Sick Children, Dublin, Ireland.
J Pediatr Orthop. 1996 Nov-Dec;16(6):731-3. doi: 10.1097/00004694-199611000-00006.
Hurler's syndrome is an autosomal recessive metabolic storage disease with distinct skeletal manifestations, which include progressive hip dislocation. Enzyme-replacement therapy by bone marrow transplantation improves life expectancy but does not prevent hip dislocation. We describe the features of hip dysplasia in a series of eight successfully engrafted patients with Hurler's syndrome. The primary pathologic condition appears to be a failure of ossification of the cartilaginous acetabulum. Five patients underwent bilateral hip-containment surgery, and all operated-on hips were reduced at a mean follow-up of 17 months. Innominate osteotomy would appear to be an essential part of the surgical procedure.
胡勒氏综合征是一种常染色体隐性代谢性贮积病,具有独特的骨骼表现,其中包括进行性髋关节脱位。通过骨髓移植进行的酶替代疗法可提高预期寿命,但无法预防髋关节脱位。我们描述了一系列8例成功接受移植的胡勒氏综合征患者的髋关节发育不良特征。主要病理状况似乎是软骨髋臼骨化失败。5例患者接受了双侧髋关节包容手术,在平均17个月的随访中,所有接受手术的髋关节均已复位。无名骨截骨术似乎是手术过程的重要组成部分。