Samuels M P, McClaughlin W, Jacobson R R, Poets C F, Southall D P
Department of Paediatrics, Royal Brompton Hospital, London.
Arch Dis Child. 1992 Feb;67(2):162-70. doi: 10.1136/adc.67.2.162.
Imposed upper airway obstruction was diagnosed as the cause of recurrent and severe cyanotic episodes in 14 patients. Episodes started between 0.8 and 33 months of age (median 1.4) and occurred over a period of 0.8 to 20 months (median 3.5). Diagnosis was made by covert video surveillance, instituted after either (a) the observation that episodes began only in the presence of one person, or (b) characteristic findings on physiological recordings, lasting between 12 hours and three weeks, performed in hospital or at home. Surveillance was undertaken for between 15 minutes and 12 days (median 24 hours) and resulted in safety for the patient and psychiatric assessment of the parent: mother (n = 12), father (n = 1), and grandmother (n = 1). These revealed histories of sexual, physical, or emotional abuse (n = 11), self harm (n = 9), factitious illness (n = 7), eating disorder (n = 10), and previous involvement with a psychiatrist (n = 7). Management of the abusing parents is complex, but recognition of their psychosocial characteristics may allow earlier diagnosis. Imposed upper airway obstruction should be considered and excluded by physiological recordings in any infant or young child with recurrent cyanotic episodes. If physiological recordings fail to substantiate a natural cause for episodes, covert video surveillance may be essential to protect the child from further injury or death.
14例患者被诊断为反复出现严重发绀发作的原因是人为造成的上气道梗阻。发作始于0.8至33个月龄(中位数为1.4),持续时间为0.8至20个月(中位数为3.5)。诊断通过隐蔽视频监控进行,在以下情况后启动:(a)观察到发作仅在有一人在场时开始;或(b)在医院或家中进行的持续12小时至3周的生理记录有特征性发现。监控持续15分钟至12天(中位数为24小时),结果保障了患者安全,并对家长进行了精神评估:母亲(n = 12)、父亲(n = 1)和祖母(n = 1)。这些家长揭示了性虐待、身体虐待或情感虐待史(n = 11)、自残史(n = 9)、人为疾病史(n = 7)、饮食失调史(n = 10)以及之前曾与精神科医生接触史(n = 7)。虐待父母的管理很复杂,但识别他们的社会心理特征可能有助于早期诊断。对于任何反复出现发绀发作的婴幼儿,应考虑人为造成的上气道梗阻并通过生理记录进行排除。如果生理记录未能证实发作的自然原因,隐蔽视频监控对于保护儿童免受进一步伤害或死亡可能至关重要。