Bachrati Csanád Z, Hickson Ian D
Cancer Research UK Laboratories, Weatherall Institute of Molecular Medicine, Unviersity of Oxford, John Radcliffe Hospital, Oxford, United Kingdom.
Methods Enzymol. 2006;409:86-100. doi: 10.1016/S0076-6879(05)09005-1.
The RecQ family of DNA helicases is highly conserved in evolution from bacteria to mammals. There are five human RecQ family members (RECQ1, BLM, WRN, RECQ4 and RECQ5), defects, three of which give rise to inherited human disorders. Mutations of BLM have been identified in patients with Bloom's syndrome, WRN has been shown to be mutated in Werner's syndrome, while mutations of RECQ4 have been associated with at least a subset of cases of both Rothmund-Thomson syndrome and RAPADILINO. The most characteristic features of these diseases are a predisposition to the development of malignancies of different types (particularly in Bloom's syndrome), some aspects of premature aging (particularly in Werner's syndrome), and on the cellular level, genome instability. In order to gain understanding of the molecular defects underlying these diseases, many laboratories have focused their research on a study of the biochemical properties of human RecQ helicases, particularly those associated with disease, and of RecQ proteins from other organisms (e.g., Sgs1p of budding yeast, Rqh1p of fission yeast, and RecQ of E.coli). In this chapter, we summarize the assay systems that we employ to analyze the catalytic properties of the BLM helicase. We have successfully used these methods for the study of other RecQ and non-RecQ helicases, indicating that they are likely to be applicable to all helicases.
DNA解旋酶的RecQ家族在从细菌到哺乳动物的进化过程中高度保守。人类RecQ家族有五个成员(RECQ1、BLM、WRN、RECQ4和RECQ5),其中三个成员的缺陷会导致人类遗传性疾病。已在布卢姆综合征患者中鉴定出BLM突变,在沃纳综合征患者中发现WRN发生突变,而RECQ4突变与罗斯蒙德-汤姆森综合征和RAPADILINO的至少一部分病例有关。这些疾病最典型的特征是易患不同类型的恶性肿瘤(尤其是在布卢姆综合征中)、一些早衰方面(尤其是在沃纳综合征中),以及在细胞水平上的基因组不稳定。为了了解这些疾病背后的分子缺陷,许多实验室将研究重点放在了对人类RecQ解旋酶,特别是与疾病相关的解旋酶,以及来自其他生物体的RecQ蛋白(如芽殖酵母的Sgslp、裂殖酵母的Rqh1p和大肠杆菌的RecQ)的生化特性研究上。在本章中,我们总结了用于分析BLM解旋酶催化特性的检测系统。我们已成功地将这些方法用于研究其他RecQ和解旋酶,这表明它们可能适用于所有解旋酶。