Kudou Megumi, Kobayashi Yoshiki, Yamashita Kenzo, Kita Hideo, Yasuba Hirotaka, Hamada Kazuyuki
Department of Respiratory Medicine, Takatsuki Red Cross Hospital.
Nihon Kokyuki Gakkai Zasshi. 2006 Jun;44(6):474-8.
Here we report two cases of congenital myopathy visited our hospital with respiratory failure. Case 1 was a 31-year-old woman, who had muscular weakness from birth but had never been diagnosed. She had an onset of pneumonia followed by severe type 2 respiratory failure. Even after the healing of pneumonia, hypercapnia remained. A diagnosis of nemaline myopathy was made after muscle biopsy. Case 2 is a 62-year-old man, who had slowly progressing respiratory failure accompanied with severe hypercapnea. His respiratory failure was improved by NIPPV. He also under went muscle biopsy and nemaline myopathy was diagnosed. Nemaline myopathy is one of congenital myopathy and is known to be a nonprogressive or slowly progressive disorder. However, some patients are diagnosed appropriately only when adult onset acute respiratory failure occurs.
在此,我们报告两例因呼吸衰竭前来我院就诊的先天性肌病病例。病例1为一名31岁女性,自出生起即有肌肉无力症状,但从未被诊断过。她因肺炎发作,随后出现严重的Ⅱ型呼吸衰竭。即使肺炎治愈后,高碳酸血症仍持续存在。肌肉活检后诊断为杆状体肌病。病例2是一名62岁男性,患有缓慢进展的呼吸衰竭并伴有严重高碳酸血症。无创正压通气改善了他的呼吸衰竭。他也接受了肌肉活检,被诊断为杆状体肌病。杆状体肌病是先天性肌病之一,已知是一种非进行性或缓慢进展性疾病。然而,一些患者仅在成年后发生急性呼吸衰竭时才得到正确诊断。