Dam Anika H D M, Koscinski Isabelle, Kremer Jan A M, Moutou Celine, Jaeger Anne-Sophie, Oudakker Astrid R, Tournaye Herman, Charlet Nicolas, Lagier-Tourenne Clotilde, van Bokhoven Hans, Viville Stephane
Centre for Reproduction, Department of Obstetrics and Gynecology, Radboud University Nijmegen Medical Centre, Nijmegen, The Netherlands.
Am J Hum Genet. 2007 Oct;81(4):813-20. doi: 10.1086/521314. Epub 2007 Aug 21.
Globozoospermia is a rare (incidence <0.1% in male infertile patients) form of teratozoospermia, mainly characterized by round-headed spermatozoa that lack an acrosome. It originates from a disturbed spermiogenesis, which is expected to be induced by a genetic factor. Several family cases and recessive mouse models with the same phenotype support this expectation. In this study, we present a consanguineous family with three affected brothers, in whom we have identified a homozygous mutation in the spermatogenesis-specific gene SPATA16. This is the first example of a nonsyndromic male infertility condition in humans caused by an autosomal gene defect, and it could also mean that the identification of other partners like SPATA16 could elucidate acrosome formation.
圆头精子症是一种罕见的(在男性不育患者中发病率<0.1%)畸形精子症,主要特征是精子头部呈圆形且缺乏顶体。它源于精子发生紊乱,推测是由遗传因素诱发的。几例家族病例以及具有相同表型的隐性小鼠模型支持了这一推测。在本研究中,我们展示了一个有三名患病兄弟的近亲家族,在该家族中我们鉴定出了精子发生特异性基因SPATA16中的纯合突变。这是人类中由常染色体基因缺陷导致的非综合征性男性不育症的首个实例,这也可能意味着鉴定出像SPATA16这样的其他相关基因可以阐明顶体的形成。