Gautier Clement A, Kitada Tohru, Shen Jie
Center for Neurologic Diseases, Brigham and Women's Hospital, Program in Neuroscience, Harvard Medical School, Boston, MA 02115, USA.
Proc Natl Acad Sci U S A. 2008 Aug 12;105(32):11364-9. doi: 10.1073/pnas.0802076105. Epub 2008 Aug 7.
Parkinson's disease (PD) is a common neurodegenerative disorder thought to be associated with mitochondrial dysfunction. Loss of function mutations in the putative mitochondrial protein PINK1 (PTEN-induced kinase 1) have been linked to familial forms of PD, but the relation of PINK1 to mammalian mitochondrial function remains unclear. Here, we report that germline deletion of the PINK1 gene in mice significantly impairs mitochondrial functions. Quantitative electron microscopic studies of the striatum in PINK1(-/-) mice at 3-4 and 24 months revealed no gross changes in the ultrastructure or the total number of mitochondria, although the number of larger mitochondria is selectively increased. Functional assays showed impaired mitochondrial respiration in the striatum but not in the cerebral cortex at 3-4 months of age, suggesting specificity of this defect for dopaminergic circuitry. Aconitase activity associated with the Krebs cycle is also reduced in the striatum of PINK1(-/-) mice. Interestingly, mitochondrial respiration activities in the cerebral cortex are decreased in PINK1(-/-) mice at 2 years compared with control mice, indicating that aging can exacerbate mitochondrial dysfunction in these mice. Furthermore, mitochondrial respiration defects can be induced in the cerebral cortex of PINK1(-/-) mice by cellular stress, such as exposure to H(2)O(2) or mild heat shock. Together, our findings demonstrate that mammalian PINK1 is important for mitochondrial function and provides critical protection against both intrinsic and environmental stress, suggesting a pathogenic mechanism by which loss of PINK1 may lead to nigrostriatal degeneration in PD.
帕金森病(PD)是一种常见的神经退行性疾病,被认为与线粒体功能障碍有关。假定的线粒体蛋白PINK1(PTEN诱导激酶1)的功能丧失突变已与家族性PD形式相关,但PINK1与哺乳动物线粒体功能的关系仍不清楚。在这里,我们报告小鼠中PINK1基因的种系缺失显著损害线粒体功能。对3至4个月和24个月大的PINK1(-/-)小鼠纹状体进行的定量电子显微镜研究显示,线粒体的超微结构或总数没有明显变化,尽管较大线粒体的数量选择性增加。功能测定表明,3至4个月大时,纹状体中的线粒体呼吸受损,但大脑皮层未受损,这表明这种缺陷对多巴胺能神经回路具有特异性。与克雷布斯循环相关的乌头酸酶活性在PINK1(-/-)小鼠的纹状体中也降低。有趣的是,与对照小鼠相比,2岁时PINK1(-/-)小鼠大脑皮层中的线粒体呼吸活性降低,这表明衰老会加剧这些小鼠的线粒体功能障碍。此外,通过细胞应激,如暴露于H2O2或轻度热休克,可在PINK1(-/-)小鼠的大脑皮层中诱导线粒体呼吸缺陷。总之,我们的研究结果表明,哺乳动物PINK1对线粒体功能很重要,并能提供针对内在和环境应激的关键保护,提示了一种PINK1缺失可能导致PD中黑质纹状体变性的致病机制。