Davidoff A M, Thompson C V, Grimm J M, Shorter N A, Filston H C, Oakes W J
Department of Surgery, Duke University Medical Center, Durham, NC 27710.
J Pediatr Surg. 1991 Aug;26(8):1001-5. doi: 10.1016/0022-3468(91)90851-j.
Recent reports have suggested an association between congenital anorectal anomalies and occult spinal dysraphism. Eighty-seven patients with anal agenesis have been treated at this institution over the last 14 years. Two of these patients had spinal cord anomalies recognized at birth (a myelomeningocele and a tethered spinal cord). Two additional patients presented with progressive neurologic deficits in early childhood and were each found to have a tethered spinal cord. To further assess the magnitude of this problem, we have used magnetic resonance imaging (MRI) of the spine to survey prospectively 23 infants with anal agenesis. Twenty-one former patients who were asymptomatic were recalled and also studied. Four of 44 patients (9%) were found to have significant occult spinal dysraphism; each child had undergone neurosurgical operation without morbidity. MRI found each child to have a tethered spinal cord, either as an isolated lesion (2) or in association with a syrinx (1) or lipomyelomeningocele (1). One of these patients had a neurologic deficit detected on careful preoperative evaluation. The other three, two of whom were less than 2 years old, had no detectable deficit. Neither the extent of the anorectal malformation, the absence of associated congenital anomalies, nor the demonstration of normal vertebral anatomy on plain radiographs of the spine precluded the presence of occult spinal dysraphism. Therefore, we recommend that all patients with anorectal anomalies undergo MRI imaging of their spines during initial evaluation to screen for occult spinal dysraphism. In addition, consideration should be given to recalling older patients for MRI evaluation.
最近的报告表明先天性肛门直肠畸形与隐性脊柱裂之间存在关联。在过去14年里,该机构共治疗了87例肛门闭锁患者。其中2例患者在出生时就被发现有脊髓异常(1例脊髓脊膜膨出和1例脊髓栓系)。另外2例患者在幼儿期出现进行性神经功能缺损,经检查均发现有脊髓栓系。为了进一步评估这一问题的严重程度,我们对23例肛门闭锁婴儿进行了脊柱磁共振成像(MRI)前瞻性检查。还召回了21例无症状的既往患者并进行了检查。44例患者中有4例(9%)被发现有明显的隐性脊柱裂;每个孩子都接受了神经外科手术,且未出现并发症。MRI检查发现每个孩子都有脊髓栓系,要么是孤立性病变(2例),要么与脊髓空洞症(1例)或脂肪脊髓脊膜膨出(1例)相关。其中1例患者在术前仔细评估时发现有神经功能缺损。另外3例,其中2例年龄小于2岁,未发现有可检测到的缺损。无论是肛门直肠畸形的程度、是否存在相关先天性异常,还是脊柱X线平片显示椎体解剖结构正常,均不能排除隐性脊柱裂的存在。因此,我们建议所有肛门直肠畸形患者在初次评估时均应接受脊柱MRI检查,以筛查隐性脊柱裂。此外,应考虑召回年龄较大的患者进行MRI评估。