Pathologisches Institut, Universitätsmedizin Mannheim, Theodor-Kutzer-Ufer 1-3, Mannheim, Germany.
Genes Chromosomes Cancer. 2010 May;49(5):471-9. doi: 10.1002/gcc.20757.
Reciprocal RARA-PML transcripts are not detected in approximately 25% of patients with PML-RARA positive acute promyelocytic leukemia (APL), but the reasons for this are poorly understood. We studied 21 PML-RARA positive/RARA-PML negative cases by bubble PCR and multiplex long template PCR to identify the genomic breakpoints. Additional RT-PCR analysis was performed based on the DNA findings. Three cases were found to have complex rearrangements involving a third locus: the first had a PML-CDC6-RARA forward DNA fusion and expressed a chimeric PML-CDC6-RARA mRNA in addition to a PML-RARA. The other two had HERC1-PML and NT_009714.17-PML genomic fusion sequences at their respective reciprocal breakpoints. Six patients were falsely classified as RARA-PML negative due to deletions on chromosome 15 and/or 17, or alternative splicing leading to atypical RARA-PML fusion transcripts, which were not identified by conventional RT-PCR assays. This study demonstrates that the frequency of RARA-PML expression has been underestimated and highlights remarkable complexity at chromosomal breakpoint regions in APL even in cases with an apparently simple balanced t(15;17)(q24;q12).
在约 25%的 PML-RARA 阳性急性早幼粒细胞白血病 (APL) 患者中未检测到相互的 RARA-PML 转录本,但原因尚不清楚。我们通过泡式 PCR 和多重长模板 PCR 研究了 21 例 PML-RARA 阳性/RARA-PML 阴性病例,以确定基因组的断裂点。根据 DNA 检测结果进行了额外的 RT-PCR 分析。发现有 3 例存在涉及第三个基因座的复杂重排:第一例有 PML-CDC6-RARA 正向 DNA 融合,并表达除 PML-RARA 之外的嵌合 PML-CDC6-RARA mRNA。另外两例在相应的反向断裂点处具有 HERC1-PML 和 NT_009714.17-PML 基因组融合序列。由于 15 号和/或 17 号染色体缺失或导致非典型 RARA-PML 融合转录本的选择性剪接,有 6 例患者被错误地归类为 RARA-PML 阴性,这些转录本未通过常规 RT-PCR 检测到。本研究表明,RARA-PML 的表达频率被低估了,即使在明显简单平衡的 t(15;17)(q24;q12)病例中,APL 中染色体断裂点区域也存在显著的复杂性。