Department of Medicine (Neurology and Rheumatology), Shinshu University School of Medicine, Matsumoto, Japan.
J Hum Genet. 2010 Apr;55(4):259-61. doi: 10.1038/jhg.2010.18. Epub 2010 Mar 19.
Fabry's disease is an X-linked lysosomal storage disorder resulting from alpha-galactosidase A deficiency. Although ischemic stroke is recognized as an important manifestation of Fabry's disease, hemorrhagic stroke is considered to be rare. Here, we report our recent clinical experience with three hemizygous male patients with Fabry's disease who developed cerebral hemorrhage. One patient had classic type Fabry's disease with p.Ala37Val mutation and others had cerebrovascular variant with p.Glu66Gln mutation. Degeneration of the cerebral small arteries secondary to deposition of glycosphingolipids and aging, in addition to hypertension and antiplatelet/anticoagulant agents, are considered to be contributing factors for hemorrhage. Fabry's disease is frequently associated with not only ischemic but also hemorrhagic stroke, especially in elderly patients.
法布瑞氏病是一种 X 连锁溶酶体贮积症,由α-半乳糖苷酶 A 缺乏引起。尽管缺血性卒中已被认为是法布瑞氏病的重要表现之一,但出血性卒中则较为罕见。在此,我们报告了最近遇到的 3 例伴有法布瑞氏病的半合子男性患者发生脑出血的临床经验。1 例患者为经典型法布瑞氏病,携带 p.Ala37Val 突变,另外 2 例为脑血管变异型,携带 p.Glu66Gln 突变。除高血压和抗血小板/抗凝药物外,推测继发于神经鞘糖脂沉积的脑小动脉变性和老化也是导致出血的因素。法布瑞氏病不仅常与缺血性卒中相关,也与出血性卒中相关,尤其是在老年患者中。