Buinauskaite Evelina, Buinauskiene Jurate, Kucinskiene Vesta, Strazdiene Dale, Valiukeviciene Skaidra
Department of Skin and Venereal Diseases, Kaunas University of Medicine, Kaunas, Lithuania.
Pediatr Dermatol. 2010 Sep-Oct;27(5):492-5. doi: 10.1111/j.1525-1470.2010.01261.x. Epub 2010 Aug 27.
Incontinentia pigmenti, also known as Bloch-Sulzberger syndrome, is a hereditary, X-linked dominant disorder characterized by abnormalities of skin, hair, teeth, eyes, and the central nervous system. It is classically considered a male-lethal disorder leading to recurrent miscarriages of male fetuses. We report a rare case of a surviving baby boy with the classic clinical features of incontinentia pigmenti that can be explained by Klinefelter syndrome.
色素失禁症,又称布洛赫-苏尔茨贝格综合征,是一种遗传性X连锁显性疾病,其特征为皮肤、毛发、牙齿、眼睛及中枢神经系统异常。传统上认为这是一种男性致死性疾病,可导致男性胎儿反复流产。我们报告了一例罕见的存活男婴病例,其具有色素失禁症的典型临床特征,这可用克兰费尔特综合征来解释。