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在一例Hughes-Stovin综合征患者中使用Amplatzer血管封堵器栓塞肺动脉瘤:病例报告

Use of an amplatzer vascular plug in embolization of a pulmonary artery aneurysm in a case of hughes-stovin syndrome: a case report.

作者信息

Tzilalis Vasileios D, Vourliotakis Georgios, Tsironis Ioannis A, Tsiligiris Vasileios D, Brountzos Elias N

机构信息

Division of Vascular Surgery, Department of Surgery, 401 General Military Hospital of Athens, Kanelopoulou Street and Mesogion Avenue, 11525 Athens, Greece.

出版信息

J Med Case Rep. 2011 Sep 1;5:425. doi: 10.1186/1752-1947-5-425.

Abstract

INTRODUCTION

Hughes-Stovin syndrome is a rare condition characterized by peripheral deep venous thrombosis accompanied by single or multiple pulmonary arterial aneurysms. The limited number of cases has precluded controlled studies of the management of pulmonary artery aneurysms, which usually cause massive hemoptysis leading to death. This is the first report of a new endovascular treatment of a single large pulmonary arterial aneurysm.

CASE PRESENTATION

An 18-year-old Caucasian man was referred to our department with recurrent severe hemoptysis. His medical history included Hughes-Stovin syndrome diagnosed during a recent hospital admission. The patient was initially treated with corticosteroids. Because of his recurrent hemoptysis, we decided to embolize a 3.5 cm pulmonary arterial aneurysm using an Amplatzer Vascular Plug. The procedure was not complicated, and the patient's post-intervention course was uneventful. The patient has remained free from any complications of the embolization 36 months after the procedure.

CONCLUSION

Percutaneous embolization of a single large pulmonary artery aneurysm with an Amplatzer Vascular Plug in a patient with Hughes-Stovin syndrome is a less invasive procedure that represents the best multidisciplinary approach in treating these patients.

摘要

引言

休斯-斯托文综合征是一种罕见疾病,其特征为外周深静脉血栓形成并伴有单个或多个肺动脉瘤。病例数量有限使得对肺动脉瘤治疗的对照研究难以开展,肺动脉瘤通常会导致大量咯血并致死。本文首次报道了一种针对单个大型肺动脉瘤的新型血管内治疗方法。

病例介绍

一名18岁的白种男性因反复严重咯血转诊至我科。他的病史包括近期住院期间诊断出的休斯-斯托文综合征。该患者最初接受了皮质类固醇治疗。由于他反复咯血,我们决定使用Amplatzer血管封堵器栓塞一个3.5厘米的肺动脉瘤。手术过程无并发症,患者术后恢复顺利。术后36个月,患者未出现栓塞的任何并发症。

结论

在患有休斯-斯托文综合征的患者中,使用Amplatzer血管封堵器对单个大型肺动脉瘤进行经皮栓塞是一种侵入性较小的手术,是治疗这些患者的最佳多学科方法。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/3858/3184110/5d5864ad7fb7/1752-1947-5-425-1.jpg

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