Department of Radiology, Bezmialem Vakif University School of Medicine, Vatan Street, Aksaray, Istanbul, Turkey.
Jpn J Radiol. 2012 Jul;30(6):522-5. doi: 10.1007/s11604-012-0079-2. Epub 2012 Apr 3.
Maple syrup urine disease (MSUD) is caused by a genetic defect of branched-chain amino acids, which include leucine, isoleucine and valine. We report diffusion-weighted imaging (DWI) findings in a newborn child with MSUD who presented with acute metabolic encephalopathic crisis. DWI (b = 1,000 s/mm(2)) showed high signal localized within the myelinated white matter (WM) areas including the cerebellar white matter, pons, bulbus, cerebral peduncles, lentiform nucleus, posterior limbs of the internal capsules, corona radiata and bilateral perirolandic cortex. The apparent diffusion coefficient values of these regions were markedly low in the affected areas. The presence of these findings was considered cytotoxic or intramyelinic edema evidenced by restricted water diffusion. In conclusion, our findings suggest that during the acute phase and early encephalopathic crisis stage of MSUD, DWI can demonstrate the involvement of myelinated WM in newborns.
枫糖尿症(MSUD)是由支链氨基酸(亮氨酸、异亮氨酸和缬氨酸)的遗传缺陷引起的。我们报告了一例 MSUD 新生儿出现急性代谢性脑病危象时的弥散加权成像(DWI)结果。DWI(b = 1000 s/mm²)显示高信号定位于包括小脑白质、脑桥、延髓、大脑脚、豆状核、内囊后肢、放射冠和双侧额顶叶皮质在内的髓鞘化白质(WM)区域。受影响区域的表观扩散系数值明显降低。这些发现的存在被认为是细胞毒性或髓鞘内水肿的证据,表现为水扩散受限。总之,我们的发现表明,在 MSUD 的急性阶段和早期脑病危象阶段,DWI 可以显示新生儿髓鞘 WM 的受累情况。