Department of Medicine II, Saarland University Medical Center, Homburg, Germany.
Ann Hepatol. 2012 Sep-Oct;11(5):710-4.
Hepatitis A virus (HAV) infection resolves in most patients uneventfully within weeks from the onset of the disease. In rare cases, however, it may relapse or cause prolonged cholestasis. Here we present a case of a 36-year-old female patient who developed severe pruritus and jaundice three weeks after initially uncomplicated hepatitis A. A relapse of the infection was excluded. Since therapy with colestyramin, antihistaminics, naloxon and ursodeoxycholic acid (UDCA) did not improve symptoms, we decided to perform plasma absorption and to start rifampicin therapy. Under these measures, pruritus and jaundice, as well as serum bilirubin levels improved gradually and after four plasmapheresis sessions we were able to discharge the patient. Genetic testing showed the presence of two procholestatic polymorphisms, the c.3084 [GG] variant within the gene encoding the hepatocanalicular bile salt transporter ABCB11 and the c.711 [AT] variant of the phosphatidylcholine floppase ABCB4. We speculate that this compound ABCB4-ABCB11 genotype led to a severe intrahepatic cholestasis in the setting of HAV infection. In conclusion, our case suggests that polymorphisms within the hepatocanalicular transporters may contribute to a more pronounced course of HAV infection. Although dedicated studies in large cohorts of patients are needed to confirm this observation, we speculate that patients carrying procholestatic hepatobiliary transporter variants may benefit from vaccination against hepatitis A.
甲型肝炎病毒(HAV)感染在大多数患者中,疾病发作后数周内会顺利痊愈。然而,在极少数情况下,HAV 可能会复发或导致长期胆汁淤积。在此,我们报告一例 36 岁女性患者,在最初无并发症的甲型肝炎发作后三周出现严重瘙痒和黄疸。排除了感染复发的可能。由于胆盐树脂、抗组胺药、纳洛酮和熊去氧胆酸(UDCA)的治疗并未改善症状,我们决定进行血浆吸收并开始利福平治疗。在这些措施下,瘙痒和黄疸以及血清胆红素水平逐渐改善,经过四次血浆置换后,我们能够出院。基因检测显示存在两种促进胆汁淤积的突变,即编码胆小管胆汁盐转运体 ABCB11 的基因 c.3084 [GG] 变体和 ABCB4 磷脂 floppase 的 c.711 [AT] 变体。我们推测这种 ABCB4-ABCB11 基因型导致了甲型肝炎病毒感染时严重的肝内胆汁淤积。总之,我们的病例提示,胆小管转运体中的突变可能导致甲型肝炎病毒感染的病程更为严重。尽管需要在大样本患者队列中进行专门的研究来证实这一观察结果,但我们推测携带促进胆汁淤积的肝胆转运体突变的患者可能受益于甲型肝炎疫苗接种。