Immune and Gene Therapy Laboratory, Department of Oncology and Pathology, Cancer Centre Karolinska, Karolinska Institutet, Stockholm, Sweden.
Exp Hematol. 2013 Jul;41(7):615-26. doi: 10.1016/j.exphem.2013.03.008. Epub 2013 Mar 30.
Telomerase activity and telomere length (TL) are prognostic markers in chronic lymphocytic leukemia (CLL). The rate-limiting component of telomerase is human telomerase reverse transcriptase (hTERT), for which multiple transcripts exist. Two splicing sites, α and β, have been described that generate deleted transcripts. Only the full-length (FL; α⁺β⁺) transcript translates into a functional protein. The aim of this work was to characterize hTERT splice variants in CLL in relation to disease activity, clinical stage, immunoglobulin heavy chain variable (IGHV) genes mutational status, and TL. Real-time polymerase chain reaction assays were validated for quantification of the hTERT transcripts with either α deletion (del-α; α⁻β⁺)), β deletion (del-β; α⁺β⁻) or both α and β deletions (del-αβ; α⁻β⁻). The splice variant expression pattern was studied in 97 patients with CLL, 6 healthy control subjects, and one CD34 cell sample. TL was assessed with real-time polymerase chain reaction in 71 of 97 samples. Thirty-two percent of the cases did not express any of the splice variants. Average FL expression was 5.5-fold higher in IGHV-unmutated (n = 35) compared with mutated (n = 59) patients (p < 0.0001). FL levels correlated directly with the percentage of IGHV homology (r = 0.34; p = 0.0007) and inversely with TL (r = -0.44; p = 0.0001). Overall, FL expression correlated significantly with that of the other splice variants. All transcripts were more frequently expressed in progressive compared with nonprogressive patients (p < 0.0001 for FL and del-α; p = 0.01 for del-β; and p = 0.006 for del-αβ). This study provides a detailed insight into the hTERT transcript pattern in CLL, highlighting the necessity of subgrouping patients according to IGHV mutation status when analyzing hTERT expression.
端粒酶活性和端粒长度 (TL) 是慢性淋巴细胞白血病 (CLL) 的预后标志物。端粒酶的限速成分是人端粒酶逆转录酶 (hTERT),它存在多种转录本。已经描述了两个剪接位点,α 和 β,它们产生缺失的转录本。只有全长 (FL; α⁺β⁺) 转录本才能翻译成具有功能的蛋白质。本研究旨在描述 CLL 中端粒酶剪接变体与疾病活动度、临床分期、免疫球蛋白重链可变区 (IGHV) 基因突变状态和 TL 的关系。通过实时聚合酶链反应 (PCR) 测定对 hTERT 转录本进行了验证,这些转录本具有 α 缺失 (del-α; α⁻β⁺)、β 缺失 (del-β; α⁺β⁻) 或两者都缺失 (del-αβ; α⁻β⁻)。研究了 97 例 CLL 患者、6 例健康对照者和 1 例 CD34 细胞样本中的剪接变体表达模式。在 71 例样本中通过实时 PCR 评估了 TL。32%的病例未表达任何剪接变体。IGHV 未突变 (n = 35) 患者的 FL 平均表达水平比突变 (n = 59) 患者高 5.5 倍 (p < 0.0001)。FL 水平与 IGHV 同源性百分比直接相关 (r = 0.34;p = 0.0007),与 TL 呈负相关 (r = -0.44;p = 0.0001)。总体而言,FL 表达与其他剪接变体显著相关。与非进行性患者相比,进展性患者更常表达所有转录本 (FL 和 del-α;p < 0.0001;del-β;p = 0.01;del-αβ;p = 0.006)。本研究深入了解了 CLL 中端粒酶转录本的模式,强调在分析 hTERT 表达时,根据 IGHV 突变状态对患者进行分组的必要性。