Chu Katrina F, Sullivan Stephen R, Taylor Helena O
Warren Alpert Medical School of Brown University.
Eplasty. 2013 Oct 3;13:e52. eCollection 2013.
Posterior vault remodeling by distraction osteogenesis is a relatively new technique used for initial correction of turribrachycephaly in children with bicoronal craniosynostosis. We present a new potential complication from this procedure; a case of pan-suture synostosis subsequent to posterior vault distraction.
We report an infant girl who presented with bicoronal synostosis in the setting of Saethre-Chotzen syndrome. She underwent posterior vault distraction and was distracted a total of 34 millimeters, with successful osteogenesis at the site.
One year postoperatively, the patient was found to have incidental, asymptomatic pan-suture synostosis on computed tomography.
To our knowledge, this is the first reported case of delayed craniosynostosis after posterior vault distraction in the literature. The possible pathogenesis and significance of this case are discussed with a review of the current literature.
通过牵张成骨进行后颅穹隆重塑是一种相对较新的技术,用于初步矫正双冠状缝早闭儿童的短头畸形。我们报告了该手术一种新的潜在并发症;1例后颅穹隆牵张后出现全颅缝早闭的病例。
我们报告了一名患有塞特勒-乔岑综合征并伴有双冠状缝早闭的女婴。她接受了后颅穹隆牵张,总共牵张了34毫米,该部位成骨成功。
术后一年,计算机断层扫描发现该患者偶然出现无症状的全颅缝早闭。
据我们所知,这是文献中首次报道的后颅穹隆牵张后迟发性颅缝早闭病例。结合当前文献综述讨论了该病例可能的发病机制及意义。