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衰老和肌肉萎缩症以区域依赖的方式对小鼠咽肌产生不同影响。

Ageing and muscular dystrophy differentially affect murine pharyngeal muscles in a region-dependent manner.

作者信息

Randolph Matthew E, Luo Qingwei, Ho Justin, Vest Katherine E, Sokoloff Alan J, Pavlath Grace K

机构信息

Department of Pharmacology, Emory University, Atlanta, GA 30322, USA.

Department of Physiology, Emory University, Atlanta, GA 30322, USA.

出版信息

J Physiol. 2014 Dec 1;592(23):5301-15. doi: 10.1113/jphysiol.2014.280420. Epub 2014 Oct 17.

Abstract

The inability to swallow, or dysphagia, is a debilitating and life-threatening condition that arises with ageing or disease. Dysphagia results from neurological or muscular impairment of one or more pharyngeal muscles, which function together to ensure proper swallowing and prevent the aspiration of food or liquid into the lungs. Little is known about the effects of age or disease on pharyngeal muscles as a group. Here we show ageing affected pharyngeal muscle growth and atrophy in wild-type mice depending on the particular muscle analysed. Furthermore, wild-type mice also developed dysphagia with ageing. Additionally, we studied pharyngeal muscles in a mouse model for oculopharyngeal muscular dystrophy, a dysphagic disease caused by a polyalanine expansion in the RNA binding protein, PABPN1. We examined pharyngeal muscles of mice overexpressing either wild-type A10 or mutant A17 PABPN1. Overexpression of mutant A17 PABPN1 differentially affected growth of the palatopharyngeus muscle dependent on its location within the pharynx. Interestingly, overexpression of wild-type A10 PABPN1 was protective against age-related muscle atrophy in the laryngopharynx and prevented the development of age-related dysphagia. These results demonstrate that pharyngeal muscles are differentially affected by both ageing and muscular dystrophy in a region-dependent manner. These studies lay important groundwork for understanding the molecular and cellular mechanisms that regulate pharyngeal muscle growth and atrophy, which may lead to novel therapies for individuals with dysphagia.

摘要

吞咽困难,即无法吞咽,是一种随着年龄增长或疾病出现而导致身体衰弱且危及生命的状况。吞咽困难是由一块或多块咽肌的神经或肌肉损伤引起的,这些肌肉共同作用以确保正常吞咽并防止食物或液体误吸入肺部。目前对于年龄或疾病对咽肌整体的影响知之甚少。在此我们表明,根据所分析的特定肌肉,衰老会影响野生型小鼠的咽肌生长和萎缩。此外,野生型小鼠也会随着年龄增长而出现吞咽困难。另外,我们在眼咽型肌营养不良的小鼠模型中研究咽肌,这是一种由RNA结合蛋白PABPN1中的多聚丙氨酸扩展引起的吞咽困难疾病。我们检查了过表达野生型A10或突变型A17 PABPN1的小鼠的咽肌。突变型A17 PABPN1的过表达对腭咽肌生长的影响因其在咽内的位置而异。有趣的是,野生型A10 PABPN1的过表达可预防喉咽部与年龄相关的肌肉萎缩,并防止与年龄相关的吞咽困难的发生。这些结果表明,咽肌在区域依赖性方面受到衰老和肌肉营养不良的不同影响。这些研究为理解调节咽肌生长和萎缩的分子和细胞机制奠定了重要基础,这可能会为吞咽困难患者带来新的治疗方法。

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