Yokoi Yoshihiro, Nakamura Ippei, Kaneko Takeshi, Sawayanagi Tomoki, Watahiki Youichi, Kuroda Makoto
Yoshihiro Yokoi, Takeshi Kaneko, Tomoki Sawayanagi, Youichi Watahiki, Department of Surgery, Shinshiro Municipal Hospital, Aichi 441-1387, Japan.
World J Gastroenterol. 2015 Jan 21;21(3):1014-9. doi: 10.3748/wjg.v21.i3.1014.
Classic polyarteritis nodosa (PAN) that targets medium-sized muscular arteries and microscopic polyangiitis (MPA), characterized by inflammation of small-caliber vessels and the presence of circulating myeloperoxidase anti-neutrophil cytoplasmic antibodies (MPO-ANCA), are distinct clinicopathological entities of systemic vasculitis. A 66-year-old woman presented with fever, cholestasis and positive MPO-ANCA. Radiological examination showed a pancreatic mass compressing the bile duct. Therefore, we performed pancreatoduodenectomy. Histopathological examination revealed that necrotizing vasculitis predominantly affecting the medium-sized vessels, spared arterioles or capillaries in the pancreas, a finding consistent with PAN. Unexpectedly, renal biopsy revealed small-caliber vasculitis and glomerulonephritis, supporting MPA. The initial manifestation of a pancreatic mass associated with vasculitis has only been reported in 7 articles. Its diagnosis is challenging because no reliable clinico-radiological findings have been observed. Clinicians should be aware of such cases and early diagnosis followed by immunosuppression is mandatory. Our findings may reflect a polyangiitis overlap syndrome coexisting between pancreatic PAN and renal MPA.
经典结节性多动脉炎(PAN)累及中等大小肌性动脉,显微镜下多血管炎(MPA)以小口径血管炎症及循环髓过氧化物酶抗中性粒细胞胞浆抗体(MPO-ANCA)阳性为特征,它们是系统性血管炎不同的临床病理实体。一名66岁女性出现发热、胆汁淤积及MPO-ANCA阳性。影像学检查显示胰腺肿物压迫胆管。因此,我们实施了胰十二指肠切除术。组织病理学检查显示坏死性血管炎主要累及中等大小血管,胰腺小动脉或毛细血管未受累,这一发现符合PAN。出乎意料的是,肾活检显示小口径血管炎和肾小球肾炎,支持MPA诊断。仅7篇文献报道过胰腺肿物合并血管炎的初始表现。由于未观察到可靠的临床影像学表现,其诊断具有挑战性。临床医生应意识到此类病例,早期诊断并给予免疫抑制治疗是必要的。我们的发现可能反映了胰腺PAN和肾MPA之间共存的多血管炎重叠综合征。